Autosomal dominant dopa-responsive dystonia

disease
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Summary

Autosomal dominant dopa-responsive dystonia (MONDO:0971063) is a disease. A subtype of dopa-responsive dystonia — broader associated-gene and molecular evidence is on the parent page (see Disease family below).

At a glance

  • Prevalence: 1-9 / 1 000 000 (Europe) [Orphanet-validated]
  • Phenotypes (HPO): 34

Clinical features

Epidemiology

Prevalence records

1 prevalence record(s), Orphanet:

TypeClassValueGeographyValidation
Point prevalence1-9 / 1 000 000EuropeValidated

Signs & symptoms

Clinical features (HPO)

34 HPO clinical features (Orphanet curated; top 34 by frequency):

HPO IDTermFrequency
HP:0000365Hearing impairmentFrequent (30-79%)
HP:0000473TorticollisFrequent (30-79%)
HP:0000716DepressionFrequent (30-79%)
HP:0000739AnxietyFrequent (30-79%)
HP:0001251AtaxiaFrequent (30-79%)
HP:0001300ParkinsonismFrequent (30-79%)
HP:0001348Brisk reflexesFrequent (30-79%)
HP:0001761Pes cavusFrequent (30-79%)
HP:0001762Talipes equinovarusFrequent (30-79%)
HP:0002063RigidityFrequent (30-79%)
HP:0002066Gait ataxiaFrequent (30-79%)
HP:0002071Abnormality of extrapyramidal motor functionFrequent (30-79%)
HP:0002174Postural tremorFrequent (30-79%)
HP:0002360Sleep abnormalityFrequent (30-79%)
HP:0002395Lower limb hyperreflexiaFrequent (30-79%)
HP:0002451Limb dystoniaFrequent (30-79%)
HP:0003487Babinski signFrequent (30-79%)
HP:0003785Decreased CSF homovanillic acid concentrationFrequent (30-79%)
HP:0004373Focal dystoniaFrequent (30-79%)
HP:0008297Transient hyperphenylalaninemiaFrequent (30-79%)
HP:0012378FatigueFrequent (30-79%)
HP:0045007Abnormality of the substantia nigraFrequent (30-79%)
HP:0002067BradykinesiaOccasional (5-29%)
HP:0000666Horizontal nystagmusOccasional (5-29%)
HP:0000722Compulsive behaviorsOccasional (5-29%)
HP:0000821HypothyroidismOccasional (5-29%)
HP:0000822HypertensionOccasional (5-29%)
HP:0001370Rheumatoid arthritisOccasional (5-29%)
HP:0002166Impaired vibration sensation in the lower limbsOccasional (5-29%)
HP:0002601Paresis of extensor muscles of the big toeOccasional (5-29%)
HP:0002650ScoliosisOccasional (5-29%)
HP:0005876Progressive flexion contracturesOccasional (5-29%)
HP:0007325Generalized dystoniaOccasional (5-29%)
HP:0001249Intellectual disabilityExcluded (0%)

Identifiers

Disease identifiers

FieldValue
Canonical nameautosomal dominant dopa-responsive dystonia
Mondo IDMONDO:0971063
Orphanet98808
ICD-111143673207
GARD0027165
Is cancer (heuristic)no

Data availability: 2 cell lines.

Disease family

This is a subtype of dopa-responsive dystonia. Genetic, therapeutic, and trial evidence is largely curated at the broader-term level — see the parent page for the associated-gene cohort and molecular evidence.

Classification path: disease › human disease › disease by developmental or physiological process › metabolic diseasedopa-responsive dystoniaautosomal dominant dopa-responsive dystonia

Related subtypes (3): TH-deficient dopa-responsive dystonia, dopa-responsive dystonia due to sepiapterin reductase deficiency, dystonia, dopa-responsive, with or without hyperphenylalaninemia, autosomal recessive

Subtypes (2): dystonia 5, intellectual developmental disorder with language impairment and early-onset DOPA-responsive dystonia-parkinsonism

Genetics & variants

GWAS landscape

No GWAS associations recorded — common-variant (GWAS) studies don’t cover this disease (typical for Mendelian / rare diseases). See the curated gene cohort and Mendelian overlap below.

Variant details and genetic-evidence tiers

No tiered GWAS variants or ClinVar records for this disease.

Genes & proteins

No associated-gene cohort resolved for this disease. Atlas builds the molecular and therapeutic sections — associated genes, protein families, druggability, pathways, interactions, and drug associations — by aggregating over a disease’s associated genes (resolved via GWAS / GenCC / ClinVar / CIViC), and none resolved here. This is expected for antibody-mediated, autoimmune, or otherwise non-gene-defined conditions; the curated evidence for this disease is its clinical features, GWAS susceptibility, and clinical trials (above).

Function

No pathway enrichment — requires an associated-gene cohort.

Therapeutics

No druggable-target or therapeutic data for this disease’s cohort.

Clinical trials & evidence

Clinical trials

Clinical trials: 0.

No linked Atlas pages yet — the cross-entity mesh grows as the corpus expands.