Chronic recurrent multifocal osteomyelitis 3

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Summary

Chronic recurrent multifocal osteomyelitis 3 (MONDO:0958177) is a disease with 1 cohort gene.

At a glance

  • Cohort genes: 1
  • ClinVar variants: 1

Clinical features

No curated clinical features (Orphanet) for this disease.

Identifiers

Disease identifiers

FieldValue
Canonical namechronic recurrent multifocal osteomyelitis 3
Mondo IDMONDO:0958177
OMIM259680
GARD0026955
Is cancer (heuristic)no

Data availability: 1 ClinVar variant · 1 GenCC gene-disease record.

Disease family

Classification path: disease › human disease › disease by body system or component › musculoskeletal system disorderskeletal system disorderbone disorderbone inflammation diseaseosteomyelitischronic recurrent multifocal osteomyelitischronic recurrent multifocal osteomyelitis 3

Related subtypes (2): Majeed syndrome, sterile multifocal osteomyelitis with periostitis and pustulosis

Genetics & variants

GWAS landscape

No GWAS associations recorded — common-variant (GWAS) studies don’t cover this disease (typical for Mendelian / rare diseases). See the curated gene cohort and Mendelian overlap below.

Variant details and genetic-evidence tiers

ClinVar germline variants

1 retrieved; paginated sample, class counts are floors:

1 pathogenic

ClinVarVariant (HGVS)GeneClassificationReview
2574622NM_000877.4(IL1R1):c.391A>G (p.Lys131Glu)IL1R1Pathogenicno assertion criteria provided

Genes & proteins

Mendelian disease overlap and somatic drivers

GenCC: 1 · Orphanet: 0 · OMIM-shared: 0 · Dual-evidence (GWAS+Mendelian): 0

GenCC gene–disease validity (cohort genes)

the Disease column is the GenCC-asserted condition — a cohort gene’s strongest validity may be for a related predisposition syndrome.

GeneClassificationInheritanceDiseaseRecords
IL1R1LimitedAutosomal dominantchronic recurrent multifocal osteomyelitis 3

Cohort genes → proteins

1 cohort genes, 1 distinct canonical proteins.

Evidence partition

SubsetGenes
multi_evidence1

Cohort genes (full)

SymbolHGNCEnsemblUniProtNameEvidence
IL1R1HGNC:5993ENSG00000115594P14778Interleukin-1 receptor type 1gencc,clinvar

Cohort function summary

Lead sentence per gene, UniProt-curated.

SymbolProtein nameFunction (lead sentence)
IL1R1Interleukin-1 receptor type 1Receptor for IL1A, IL1B and IL1RN.

Protein-family classification

Druggable: 1 · Difficult: 0 · Unknown: 0 · Druggable fraction: 1.0

Family distribution

Cohort families vs a genome-wide background (hypergeometric, BH-FDR; fold = observed/expected). Counts kept; sorted by enrichment, so the catch-all Other/Unknown bucket no longer leads.

FamilyGenesFoldFDR
Antibody/Immunoglobulin129.2×0.034

Per-gene assignment

SymbolFamilyDruggable?ECInterPro (top 3)
IL1R1Antibody/ImmunoglobulinyesTIR_dom, Ig_sub, IL-1_rcpt_I/II-typ

Expression context

Cohort genes with no expression data: 0.

1 cohort gene are a single-cell marker in ≥1 SCXA experiment.

Breadth distribution (Bgee present_calls)

BucketGenes
narrow (1-5 tissues)0
moderate (6-20)0
broad (>20)1
unknown0

Top tissues across cohort

TissueCohort genes
palpebral conjunctiva1
pericardium1
tibia1

Per-gene tissue summary (top 30)

SymbolBgee breadthFANTOM5 breadthSCXATop tissues
IL1R1279ubiquitousmarkerpalpebral conjunctiva, tibia, pericardium

Protein interactions among cohort

Intra-cohort edges: 0.

Hub genes (top 10 by interactor count)

SymbolInteractor count
IL1R12,820

Structural data

PDB: 1 · AlphaFold-only: 0 · No structure: 0

Cohort genes with PDB structures (top 30)

SymbolUniProtPDB entries
IL1R1P147785

Function

Pathway analysis

Distinct Reactome pathways touched by cohort: 3. Enrichment computed across 1 evidence-associated genes (1 with Reactome annotation).

Pathways by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 1 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

PathwayCohort genesFoldFDRSample cohort genes
Interleukin-10 signaling1233.1×0.009IL1R1
Interleukin-1 signaling1124.1×0.009IL1R1
Potential therapeutics for SARS1114.2×0.009IL1R1

GO biological processes by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 1 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

GO termCohort genesFoldFDRSample cohort genes
positive regulation of interleukin-1-mediated signaling pathway116852.0×8e-04IL1R1
smooth muscle adaptation14213.0×0.001IL1R1
positive regulation of platelet-derived growth factor receptor signaling pathway13370.4×0.001IL1R1
positive regulation of neutrophil extravasation12407.4×0.001IL1R1
positive regulation of T-helper 1 cell cytokine production12106.5×0.001IL1R1
interleukin-1-mediated signaling pathway1802.5×0.003IL1R1
response to interleukin-11510.7×0.004IL1R1
positive regulation of type II interferon production1224.7×0.008IL1R1
regulation of inflammatory response1168.5×0.009IL1R1
positive regulation of phosphatidylinositol 3-kinase/protein kinase B signal transduction178.4×0.018IL1R1
positive regulation of canonical NF-kappaB signal transduction172.6×0.018IL1R1
cell surface receptor signaling pathway164.1×0.018IL1R1
immune response147.1×0.023IL1R1
inflammatory response137.7×0.027IL1R1

Therapeutics

Drug target analysis

Approved (phase 4): 0 · Phase ≥3: 0 · Phased (≥1): 0 · Undrugged: 1

Druggability breadth: 1 of 1 evidence-associated genes (100%) have a ChEMBL target (buckets above are over the deeply-mined display cohort).

Top cohort targets by molecule count

SymbolMoleculesMax phase
IL1R100

Bioactivity and enzyme data

Enzyme cohort genes (≥1 EC): 0.

Cohort genes with ChEMBL bioactivity (full, sorted by assay count)

SymbolAssaysType breakdown
IL1R111Binding:11

Pharmacogenomics

Cohort genes with a PharmGKB record: 1; with CPIC/DPWG dosing guidelines: 0.

No cohort gene has a CPIC/DPWG genotype-guided dosing guideline (PharmGKB).

Chemical tractability of cohort targets

0 approved/phased compounds have measured bioactivity against a cohort gene (and aren’t yet in disease-level trials). This is a research / tractability signal, NOT a therapeutic recommendation — a bioactivity row often reflects off-target or screening binding (e.g. promiscuous kinase inhibitors against a cohort kinase), implying no disease mechanism.

Druggability pyramid

Cohort genes binned by druggability tier (high → low):

TierDefinitionGenesSymbols
AApproved (phase 4 drug)0
BPhased (≥1) drug, not yet approved0
CDruggable family + PDB, no drug1IL1R1
DDruggable family + AlphaFold only, no drug0
EDifficult family or no structure, no drug0

Undrugged target profiles

1 cohort genes are undrugged. Ranked by ‘starting-point quality’ (assay depth + drugged-partner adjacency).

SymbolChEMBL assaysDrugged partners (top 3)
IL1R111

Clinical trials & evidence

Clinical trials

Clinical trials: 0.