Congenital anomalies of kidney and urinary tract 3

disease
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Also known as CAKUT3

Summary

Congenital anomalies of kidney and urinary tract 3 (MONDO:0032646) is a disease with 1 cohort gene.

At a glance

  • Cohort genes: 1
  • ClinVar variants: 18

Clinical features

No curated clinical features (Orphanet) for this disease.

Identifiers

Disease identifiers

FieldValue
Canonical namecongenital anomalies of kidney and urinary tract 3
Mondo IDMONDO:0032646
OMIM618270
UMLSC4748921
MedGen1648427
GARD0025711
Is cancer (heuristic)no

Also known as: CAKUT3

Data availability: 18 ClinVar variants · 1 GenCC gene-disease record.

Disease family

Classification path: disease › human disease › disease by developmental or physiological process › disorder of development or morphogenesisdevelopmental defect during embryogenesiscongenital anomaly of kidney and urinary tractcongenital anomalies of kidney and urinary tract 3

Related subtypes (2): congenital anomalies of kidney and urinary tract 1, congenital anomalies of kidney and urinary tract 2

Genetics & variants

GWAS landscape

No GWAS associations recorded — common-variant (GWAS) studies don’t cover this disease (typical for Mendelian / rare diseases). See the curated gene cohort and Mendelian overlap below.

Variant details and genetic-evidence tiers

ClinVar germline variants

18 retrieved; paginated sample, class counts are floors:

11 uncertain significance, 3 likely benign, 2 likely pathogenic, 1 benign, 1 pathogenic

ClinVarVariant (HGVS)GeneClassificationReview
548653NM_003489.4(NRIP1):c.279del (p.Asp92_Trp93insTer)NRIP1Pathogenicno assertion criteria provided
4533294NM_003489.4(NRIP1):c.2791A>T (p.Lys931Ter)NRIP1Likely pathogeniccriteria provided, single submitter
4812934NM_003489.4(NRIP1):c.3203T>C (p.Leu1068Pro)NRIP1Likely pathogenicno assertion criteria provided
1339141NM_003489.4(NRIP1):c.2227G>A (p.Glu743Lys)NRIP1Uncertain significancecriteria provided, single submitter
1339181NM_003489.4(NRIP1):c.1868C>T (p.Ala623Val)NRIP1Uncertain significancecriteria provided, single submitter
1723300NM_003489.4(NRIP1):c.3465_3468del (p.Lys1155fs)NRIP1Uncertain significancecriteria provided, multiple submitters, no conflicts
2226213NM_003489.4(NRIP1):c.860C>T (p.Thr287Met)NRIP1Uncertain significancecriteria provided, multiple submitters, no conflicts
2394795NM_003489.4(NRIP1):c.3364A>G (p.Arg1122Gly)NRIP1Uncertain significancecriteria provided, multiple submitters, no conflicts
3236105NM_003489.4(NRIP1):c.739G>A (p.Val247Met)NRIP1Uncertain significancecriteria provided, single submitter
3367024NM_003489.4(NRIP1):c.3439C>G (p.Leu1147Val)NRIP1Uncertain significancecriteria provided, single submitter
3390953NM_003489.4(NRIP1):c.1627_1628delinsTT (p.Pro543Phe)NRIP1Uncertain significancecriteria provided, single submitter
3891858NM_003489.4(NRIP1):c.3235G>C (p.Val1079Leu)NRIP1Uncertain significancecriteria provided, single submitter
4277854NM_003489.4(NRIP1):c.2837_2838del (p.Val946fs)NRIP1Uncertain significancecriteria provided, single submitter
992908NM_003489.4(NRIP1):c.1660C>T (p.Pro554Ser)NRIP1Uncertain significancecriteria provided, single submitter
1326992NM_003489.4(NRIP1):c.225G>A (p.Gly75=)NRIP1Benigncriteria provided, multiple submitters, no conflicts
2164085NM_003489.4(NRIP1):c.2038G>A (p.Ala680Thr)NRIP1Likely benigncriteria provided, multiple submitters, no conflicts
2706648NM_003489.4(NRIP1):c.2840G>A (p.Arg947Gln)NRIP1Likely benigncriteria provided, multiple submitters, no conflicts
734220NM_003489.4(NRIP1):c.3455C>T (p.Thr1152Met)NRIP1Likely benigncriteria provided, multiple submitters, no conflicts

Genes & proteins

Mendelian disease overlap and somatic drivers

GenCC: 1 · Orphanet: 0 · OMIM-shared: 0 · Dual-evidence (GWAS+Mendelian): 0

GenCC gene–disease validity (cohort genes)

the Disease column is the GenCC-asserted condition — a cohort gene’s strongest validity may be for a related predisposition syndrome.

GeneClassificationInheritanceDiseaseRecords
NRIP1LimitedAutosomal dominantcongenital anomalies of kidney and urinary tract 3

Cohort genes → proteins

1 cohort genes, 1 distinct canonical proteins.

Evidence partition

SubsetGenes
multi_evidence1

Cohort genes (full)

SymbolHGNCEnsemblUniProtNameEvidence
NRIP1HGNC:8001ENSG00000180530P48552Nuclear receptor-interacting protein 1gencc,clinvar

Cohort function summary

Lead sentence per gene, UniProt-curated.

SymbolProtein nameFunction (lead sentence)
NRIP1Nuclear receptor-interacting protein 1Modulates transcriptional activation by steroid receptors such as NR3C1, NR3C2 and ESR1.

Protein-family classification

Druggable: 0 · Difficult: 0 · Unknown: 1 · Druggable fraction: 0.0

Family distribution

Cohort families vs a genome-wide background (hypergeometric, BH-FDR; fold = observed/expected). Counts kept; sorted by enrichment, so the catch-all Other/Unknown bucket no longer leads.

FamilyGenesFoldFDR
Other/Unknown11.8×0.558

Per-gene assignment

SymbolFamilyDruggable?ECInterPro (top 3)
NRIP1Other/UnknownnoNRIP1, NRIP1_RD1, NRIP1_RD2

Expression context

Cohort genes with no expression data: 0.

1 cohort gene are a single-cell marker in ≥1 SCXA experiment.

Breadth distribution (Bgee present_calls)

BucketGenes
narrow (1-5 tissues)0
moderate (6-20)0
broad (>20)1
unknown0

Top tissues across cohort

TissueCohort genes
caput epididymis1
corpus epididymis1
jejunal mucosa1

Per-gene tissue summary (top 30)

SymbolBgee breadthFANTOM5 breadthSCXATop tissues
NRIP1294ubiquitousmarkercorpus epididymis, caput epididymis, jejunal mucosa

Protein interactions among cohort

Intra-cohort edges: 0.

Hub genes (top 10 by interactor count)

SymbolInteractor count
NRIP11,681

Structural data

PDB: 1 · AlphaFold-only: 0 · No structure: 0

Cohort genes with PDB structures (top 30)

SymbolUniProtPDB entries
NRIP1P4855217

Function

Pathway analysis

Distinct Reactome pathways touched by cohort: 7. Enrichment computed across 1 evidence-associated genes (1 with Reactome annotation).

Pathways by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 1 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

PathwayCohort genesFoldFDRSample cohort genes
NR1H2 & NR1H3 regulate gene expression linked to gluconeogenesis12284.0×0.003NRIP1
NR1H2 & NR1H3 regulate gene expression linked to lipogenesis11142.0×0.003NRIP1
RORA,B,C and NR1D1 (REV-ERBA) regulate gene expression1407.9×0.005NRIP1
Expression of BMAL (ARNTL), CLOCK, and NPAS21292.8×0.005NRIP1
SUMOylation of transcription cofactors1243.0×0.005NRIP1
Heme signaling1215.5×0.005NRIP1
Estrogen-dependent gene expression175.6×0.013NRIP1

GO biological processes by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 1 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

GO termCohort genesFoldFDRSample cohort genes
ovarian follicle rupture116852.0×4e-04NRIP1
lipid storage1543.6×0.006NRIP1
cellular response to estradiol stimulus1411.0×0.006NRIP1
circadian rhythm1244.2×0.006NRIP1
circadian regulation of gene expression1234.1×0.006NRIP1
negative regulation of transcription by RNA polymerase II117.7×0.066NRIP1
positive regulation of transcription by RNA polymerase II114.9×0.067NRIP1

Therapeutics

Drug target analysis

Approved (phase 4): 0 · Phase ≥3: 0 · Phased (≥1): 0 · Undrugged: 1

Druggability breadth: 0 of 1 evidence-associated genes (0%) have a ChEMBL target (buckets above are over the deeply-mined display cohort).

Top cohort targets by molecule count

SymbolMoleculesMax phase
NRIP100

Bioactivity and enzyme data

Enzyme cohort genes (≥1 EC): 0.

Pharmacogenomics

Cohort genes with a PharmGKB record: 1; with CPIC/DPWG dosing guidelines: 0.

No cohort gene has a CPIC/DPWG genotype-guided dosing guideline (PharmGKB).

Chemical tractability of cohort targets

0 approved/phased compounds have measured bioactivity against a cohort gene (and aren’t yet in disease-level trials). This is a research / tractability signal, NOT a therapeutic recommendation — a bioactivity row often reflects off-target or screening binding (e.g. promiscuous kinase inhibitors against a cohort kinase), implying no disease mechanism.

Druggability pyramid

Cohort genes binned by druggability tier (high → low):

TierDefinitionGenesSymbols
AApproved (phase 4 drug)0
BPhased (≥1) drug, not yet approved0
CDruggable family + PDB, no drug0
DDruggable family + AlphaFold only, no drug0
EDifficult family or no structure, no drug1NRIP1

Undrugged target profiles

1 cohort genes are undrugged. Ranked by ‘starting-point quality’ (assay depth + drugged-partner adjacency).

SymbolChEMBL assaysDrugged partners (top 3)
NRIP10

Clinical trials & evidence

Clinical trials

Clinical trials: 0.