ectodermal dysplasia 11A, hypohidrotic/hair/tooth type, autosomal dominant

disease
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Also known as ECTD11A

Summary

ectodermal dysplasia 11A, hypohidrotic/hair/tooth type, autosomal dominant (MONDO:0013982) is a disease caused by EDARADD (GenCC Strong), with 1 cohort gene.

At a glance

  • Causal gene: EDARADD (GenCC Strong)
  • Cohort genes: 1
  • ClinVar variants: 44

Clinical features

No curated clinical features (Orphanet) for this disease.

Identifiers

Disease identifiers

FieldValue
Canonical nameectodermal dysplasia 11A, hypohidrotic/hair/tooth type, autosomal dominant
Mondo IDMONDO:0013982
OMIM614940
DOIDDOID:0111653
UMLSC3541517
MedGen762105
GARD0018592
Is cancer (heuristic)no

Also known as: ECTD11A · ectodermal dysplasia 11A, hypohidrotic/hair/tooth type, autosomal dominant

Data availability: 44 ClinVar variants · 3 GenCC gene-disease records.

Disease family

Classification path: disease › human disease › disease by etiologic mechanism › disease of genetic or genomic mechanism › hereditary disease › autosomal genetic disease › autosomal dominant disease › autosomal dominant hypohidrotic ectodermal dysplasiaectodermal dysplasia 11A, hypohidrotic/hair/tooth type, autosomal dominant

Related subtypes (1): ectodermal dysplasia 10A, hypohidrotic/hair/nail type, autosomal dominant

Genetics & variants

GWAS landscape

No GWAS associations recorded — common-variant (GWAS) studies don’t cover this disease (typical for Mendelian / rare diseases). See the curated gene cohort and Mendelian overlap below.

Variant details and genetic-evidence tiers

ClinVar germline variants

44 retrieved; paginated sample, class counts are floors:

17 uncertain significance, 8 benign, 6 likely pathogenic, 5 likely benign, 4 benign/likely benign, 3 pathogenic, 1 conflicting classifications of pathogenicity

ClinVarVariant (HGVS)GeneClassificationReview
2939815NC_000001.11:g.236468231_236468234delEDARADDPathogeniccriteria provided, single submitter
4189NM_145861.4(EDARADD):c.365T>G (p.Leu122Arg)EDARADDPathogenicno assertion criteria provided
473077NM_145861.4(EDARADD):c.417G>A (p.Trp139Ter)EDARADDPathogeniccriteria provided, single submitter
1333297NM_145861.4(EDARADD):c.359A>C (p.Asp120Ala)EDARADDLikely pathogeniccriteria provided, single submitter
1347024NC_000001.10:g.(?236631511)(236631596_?)dupEDARADDLikely pathogeniccriteria provided, single submitter
253092NM_145861.4(EDARADD):c.367G>A (p.Asp123Asn)EDARADDLikely pathogeniccriteria provided, single submitter
3581597NM_145861.4(EDARADD):c.61+1G>CEDARADDLikely pathogeniccriteria provided, single submitter
4188NM_145861.4(EDARADD):c.454G>A (p.Glu152Lys)EDARADDLikely pathogeniccriteria provided, single submitter
4277299NM_145861.4(EDARADD):c.359A>T (p.Asp120Val)EDARADDLikely pathogeniccriteria provided, single submitter
843361NM_145861.4(EDARADD):c.392C>T (p.Pro131Leu)EDARADDConflicting classifications of pathogenicitycriteria provided, conflicting classifications
1055040NM_145861.4(EDARADD):c.568G>A (p.Asp190Asn)EDARADDUncertain significancecriteria provided, single submitter
1354328NM_145861.4(EDARADD):c.358_359delinsAT (p.Asp120Ile)EDARADDUncertain significancecriteria provided, single submitter
1439044NM_145861.4(EDARADD):c.446C>T (p.Ser149Phe)EDARADDUncertain significancecriteria provided, single submitter
1514540NC_000001.10:g.(?236631511)(236645949_?)dupEDARADDUncertain significancecriteria provided, single submitter
1967978NM_145861.4(EDARADD):c.22C>G (p.Gln8Glu)EDARADDUncertain significancecriteria provided, multiple submitters, no conflicts
2161136NM_145861.4(EDARADD):c.101G>A (p.Ser34Asn)EDARADDUncertain significancecriteria provided, single submitter
2188579NM_145861.4(EDARADD):c.220G>A (p.Gly74Arg)EDARADDUncertain significancecriteria provided, multiple submitters, no conflicts
2938095NM_145861.4(EDARADD):c.484A>G (p.Ser162Gly)EDARADDUncertain significancecriteria provided, single submitter
2939545NM_145861.4(EDARADD):c.154C>T (p.Pro52Ser)EDARADDUncertain significancecriteria provided, single submitter
2945599NM_145861.4(EDARADD):c.404C>T (p.Thr135Met)EDARADDUncertain significancecriteria provided, single submitter
2952473NM_145861.4(EDARADD):c.543G>T (p.Glu181Asp)EDARADDUncertain significancecriteria provided, single submitter
2952474NM_145861.4(EDARADD):c.548_549del (p.Leu182_Cys183insTer)EDARADDUncertain significancecriteria provided, single submitter
3065706NM_145861.4(EDARADD):c.80C>T (p.Pro27Leu)EDARADDUncertain significancecriteria provided, single submitter
3581599NM_145861.4(EDARADD):c.358G>C (p.Asp120His)EDARADDUncertain significancecriteria provided, multiple submitters, no conflicts
3759666NM_145861.4(EDARADD):c.53A>G (p.His18Arg)EDARADDUncertain significancecriteria provided, single submitter
540293NM_145861.4(EDARADD):c.509G>A (p.Arg170Gln)EDARADDUncertain significancecriteria provided, multiple submitters, no conflicts
572712NM_145861.4(EDARADD):c.199A>T (p.Asn67Tyr)EDARADDUncertain significancecriteria provided, single submitter
1255368NM_145861.4(EDARADD):c.62-41A>GEDARADDBenigncriteria provided, multiple submitters, no conflicts
1255369NM_145861.4(EDARADD):c.161-33G>CEDARADDBenigncriteria provided, multiple submitters, no conflicts
1293214NM_145861.4(EDARADD):c.161-6delEDARADDBenigncriteria provided, multiple submitters, no conflicts

Genes & proteins

Mendelian disease overlap and somatic drivers

GenCC: 9 · Orphanet: 3 · OMIM-shared: 0 · Dual-evidence (GWAS+Mendelian): 0

GenCC gene–disease validity (cohort genes)

the Disease column is the GenCC-asserted condition — a cohort gene’s strongest validity may be for a related predisposition syndrome.

GeneClassificationInheritanceDiseaseRecords
EDARADDStrongAutosomal dominantectodermal dysplasia 11A, hypohidrotic/hair/tooth type, autosomal dominant9

Orphanet rare-disease linkage (cohort genes)

GeneOrphanet IDRare disease
EDARADDOrphanet:1810Autosomal dominant hypohidrotic ectodermal dysplasia
EDARADDOrphanet:248Autosomal recessive hypohidrotic ectodermal dysplasia
EDARADDOrphanet:99798Oligodontia

Cohort genes → proteins

1 cohort genes, 1 distinct canonical proteins.

Evidence partition

SubsetGenes
multi_evidence1

Cohort genes (full)

SymbolHGNCEnsemblUniProtNameEvidence
EDARADDHGNC:14341ENSG00000186197Q8WWZ3Ectodysplasin-A receptor-associated adapter proteingencc,clinvar

Cohort function summary

Lead sentence per gene, UniProt-curated.

SymbolProtein nameFunction (lead sentence)
EDARADDEctodysplasin-A receptor-associated adapter proteinAdapter protein that interacts with EDAR DEATH domain and couples the receptor to EDA signaling pathway during morphogenesis of ectodermal organs.

Protein-family classification

Druggable: 0 · Difficult: 0 · Unknown: 1 · Druggable fraction: 0.0

Family distribution

Cohort families vs a genome-wide background (hypergeometric, BH-FDR; fold = observed/expected). Counts kept; sorted by enrichment, so the catch-all Other/Unknown bucket no longer leads.

FamilyGenesFoldFDR
Other/Unknown11.8×0.558

Per-gene assignment

SymbolFamilyDruggable?ECInterPro (top 3)
EDARADDOther/UnknownnoDeath_dom, DEATH-like_dom_sf, EDARADD

Expression context

Cohort genes with no expression data: 0.

1 cohort gene are a single-cell marker in ≥1 SCXA experiment.

Breadth distribution (Bgee present_calls)

BucketGenes
narrow (1-5 tissues)0
moderate (6-20)0
broad (>20)1
unknown0

Top tissues across cohort

TissueCohort genes
islet of Langerhans1
male germ line stem cell (sensu Vertebrata) in testis1
sural nerve1

Per-gene tissue summary (top 30)

SymbolBgee breadthFANTOM5 breadthSCXATop tissues
EDARADD147broadmarkerislet of Langerhans, sural nerve, male germ line stem cell (sensu Vertebrata) in testis

Protein interactions among cohort

Intra-cohort edges: 0.

Hub genes (top 10 by interactor count)

SymbolInteractor count
EDARADD659

Structural data

PDB: 0 · AlphaFold-only: 1 · No structure: 0

AlphaFold-only cohort genes (top 30 by pLDDT)

SymbolUniProtpLDDT
EDARADDQ8WWZ373.81

Function

Pathway analysis

Distinct Reactome pathways touched by cohort: 1. Enrichment computed across 1 evidence-associated genes (1 with Reactome annotation).

Pathways by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 1 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

PathwayCohort genesFoldFDRSample cohort genes
TNFs bind their physiological receptors1393.8×0.003EDARADD

GO biological processes by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 1 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

GO termCohort genesFoldFDRSample cohort genes
cell differentiation129.1×0.062EDARADD
signal transduction116.1×0.062EDARADD

Therapeutics

Drug target analysis

Approved (phase 4): 0 · Phase ≥3: 0 · Phased (≥1): 0 · Undrugged: 1

Druggability breadth: 0 of 1 evidence-associated genes (0%) have a ChEMBL target (buckets above are over the deeply-mined display cohort).

Top cohort targets by molecule count

SymbolMoleculesMax phase
EDARADD00

Bioactivity and enzyme data

Enzyme cohort genes (≥1 EC): 0.

Pharmacogenomics

Cohort genes with a PharmGKB record: 1; with CPIC/DPWG dosing guidelines: 0.

No cohort gene has a CPIC/DPWG genotype-guided dosing guideline (PharmGKB).

Chemical tractability of cohort targets

0 approved/phased compounds have measured bioactivity against a cohort gene (and aren’t yet in disease-level trials). This is a research / tractability signal, NOT a therapeutic recommendation — a bioactivity row often reflects off-target or screening binding (e.g. promiscuous kinase inhibitors against a cohort kinase), implying no disease mechanism.

Druggability pyramid

Cohort genes binned by druggability tier (high → low):

TierDefinitionGenesSymbols
AApproved (phase 4 drug)0
BPhased (≥1) drug, not yet approved0
CDruggable family + PDB, no drug0
DDruggable family + AlphaFold only, no drug0
EDifficult family or no structure, no drug1EDARADD

Undrugged target profiles

1 cohort genes are undrugged. Ranked by ‘starting-point quality’ (assay depth + drugged-partner adjacency).

SymbolChEMBL assaysDrugged partners (top 3)
EDARADD0

Clinical trials & evidence

Clinical trials

Clinical trials: 0.