factor 5 and Factor VIII, combined deficiency of, 2

disease
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Also known as combined deficiency of factor V and factor VIII caused by mutation in MCFD2F5F8D2factor 5 and Factor VIII, combined deficiency of, type 2factor V and factor VIII, combined deficiency offactor V and factor VIII, combined deficiency of, 2MCFD2 combined deficiency of factor V and factor VIII

Summary

factor 5 and Factor VIII, combined deficiency of, 2 (MONDO:0013331) is a disease caused by MCFD2 (GenCC Definitive), with 2 cohort genes.

At a glance

  • Causal gene: MCFD2 (GenCC Definitive)
  • Cohort genes: 2
  • ClinVar variants: 113

Clinical features

No curated clinical features (Orphanet) for this disease.

Identifiers

Disease identifiers

FieldValue
Canonical namefactor 5 and Factor VIII, combined deficiency of, 2
Mondo IDMONDO:0013331
OMIM613625
UMLSC3150889
MedGen462239
GARD0018632
Is cancer (heuristic)no

Also known as: combined deficiency of factor V and factor VIII caused by mutation in MCFD2 · F5F8D2 · factor 5 and Factor VIII, combined deficiency of, 2 · factor 5 and Factor VIII, combined deficiency of, type 2 · factor V and factor VIII, combined deficiency of · factor V and factor VIII, combined deficiency of, 2 · MCFD2 combined deficiency of factor V and factor VIII

Data availability: 113 ClinVar variants · 5 GenCC gene-disease records.

Disease family

Classification path: disease › human disease › disease by body system or component › hematologic disorderblood coagulation diseasecoagulation protein diseasecombined deficiency of factor V and factor VIIIfactor 5 and Factor VIII, combined deficiency of, 2

Related subtypes (2): factor V and factor VIII, combined deficiency of, type 1, factor V and factor VIII, combined deficiency of, with normal protein C and protein C inhibitor

Genetics & variants

GWAS landscape

No GWAS associations recorded — common-variant (GWAS) studies don’t cover this disease (typical for Mendelian / rare diseases). See the curated gene cohort and Mendelian overlap below.

Variant details and genetic-evidence tiers

ClinVar germline variants

113 retrieved; paginated sample, class counts are floors:

71 uncertain significance, 25 benign, 7 pathogenic, 6 likely benign, 2 likely pathogenic, 2 conflicting classifications of pathogenicity

ClinVarVariant (HGVS)GeneClassificationReview
2866NM_139279.6(MCFD2):c.309+1G>AMCFD2Pathogenicno assertion criteria provided
2867NM_139279.6(MCFD2):c.103del (p.Gln35fs)MCFD2Pathogenicno assertion criteria provided
2868NM_139279.6(MCFD2):c.249del (p.Asp83fs)MCFD2Pathogenicno assertion criteria provided
2869NM_139279.6(MCFD2):c.265_272del (p.Asp89fs)MCFD2Pathogenicno assertion criteria provided
2870NM_139279.6(MCFD2):c.387C>G (p.Asp129Glu)MCFD2Pathogenicno assertion criteria provided
2871NM_139279.6(MCFD2):c.407T>C (p.Ile136Thr)MCFD2Pathogenicno assertion criteria provided
2872NM_139279.6(MCFD2):c.241G>T (p.Asp81Tyr)MCFD2Pathogenicno assertion criteria provided
2865NM_139279.6(MCFD2):c.149+5G>AMCFD2Likely pathogeniccriteria provided, multiple submitters, no conflicts
800824NM_139279.6(MCFD2):c.47T>C (p.Leu16Pro)MCFD2Likely pathogeniccriteria provided, single submitter
336332NM_139279.6(MCFD2):c.*2848C>TMCFD2Conflicting classifications of pathogenicitycriteria provided, conflicting classifications
336385NM_139279.6(MCFD2):c.-7+11T>AMCFD2Conflicting classifications of pathogenicitycriteria provided, conflicting classifications
336392NM_001171506.2(MCFD2):c.-189C>GLOC129933675Uncertain significancecriteria provided, single submitter
896542NM_001171506.2(MCFD2):c.-205G>CLOC129933675Uncertain significancecriteria provided, single submitter
336325NM_139279.6(MCFD2):c.*3354A>GMCFD2Uncertain significancecriteria provided, single submitter
336327NM_139279.6(MCFD2):c.*3293A>CMCFD2Uncertain significancecriteria provided, single submitter
336329NM_139279.6(MCFD2):c.*3099G>AMCFD2Uncertain significancecriteria provided, single submitter
336331NM_139279.6(MCFD2):c.*3014G>AMCFD2Uncertain significancecriteria provided, single submitter
336333NM_139279.6(MCFD2):c.*2789G>CMCFD2Uncertain significancecriteria provided, single submitter
336337NM_139279.6(MCFD2):c.*2565A>GMCFD2Uncertain significancecriteria provided, single submitter
336340NM_139279.6(MCFD2):c.*2169G>AMCFD2Uncertain significancecriteria provided, single submitter
336342NM_139279.6(MCFD2):c.*2141G>CMCFD2Uncertain significancecriteria provided, single submitter
336343NM_139279.6(MCFD2):c.*2121G>AMCFD2Uncertain significancecriteria provided, single submitter
336345NM_139279.6(MCFD2):c.*2017C>TMCFD2Uncertain significancecriteria provided, single submitter
336346NM_139279.6(MCFD2):c.*1995G>AMCFD2Uncertain significancecriteria provided, single submitter
336349NM_139279.6(MCFD2):c.*1875T>CMCFD2Uncertain significancecriteria provided, single submitter
336355NM_139279.6(MCFD2):c.*1415C>TMCFD2Uncertain significancecriteria provided, single submitter
336356NM_139279.6(MCFD2):c.*1354G>TMCFD2Uncertain significancecriteria provided, single submitter
336358NM_139279.6(MCFD2):c.*1314C>TMCFD2Uncertain significancecriteria provided, single submitter
336361NM_139279.6(MCFD2):c.*1158C>AMCFD2Uncertain significancecriteria provided, single submitter
336362NM_139279.6(MCFD2):c.*1111G>CMCFD2Uncertain significancecriteria provided, single submitter

Genes & proteins

Mendelian disease overlap and somatic drivers

GenCC: 6 · Orphanet: 1 · OMIM-shared: 0 · Dual-evidence (GWAS+Mendelian): 0

GenCC gene–disease validity (cohort genes)

the Disease column is the GenCC-asserted condition — a cohort gene’s strongest validity may be for a related predisposition syndrome.

GeneClassificationInheritanceDiseaseRecords
MCFD2DefinitiveAutosomal recessivefactor 5 and Factor VIII, combined deficiency of, 26

Orphanet rare-disease linkage (cohort genes)

GeneOrphanet IDRare disease
MCFD2Orphanet:35909Combined deficiency of factor V and factor VIII

Cohort genes → proteins

2 cohort genes, 1 distinct canonical proteins.

Evidence partition

SubsetGenes
multi_evidence2

Cohort genes (full)

SymbolHGNCEnsemblUniProtNameEvidence
MCFD2HGNC:18451ENSG00000180398Q8NI22Multiple coagulation factor deficiency protein 2gencc,clinvar
MCFD2-AS1HGNC:58223ENSG00000228925MCFD2 antisense RNA 1clinvar

Cohort function summary

Lead sentence per gene, UniProt-curated.

SymbolProtein nameFunction (lead sentence)
MCFD2Multiple coagulation factor deficiency protein 2The MCFD2-LMAN1 complex forms a specific cargo receptor for the ER-to-Golgi transport of selected proteins.

Protein-family classification

Druggable: 0 · Difficult: 0 · Unknown: 2 · Druggable fraction: 0.0

Family distribution

Cohort families vs a genome-wide background (hypergeometric, BH-FDR; fold = observed/expected). Counts kept; sorted by enrichment, so the catch-all Other/Unknown bucket no longer leads.

FamilyGenesFoldFDR
Other/Unknown21.8×0.312

Per-gene assignment

SymbolFamilyDruggable?ECInterPro (top 3)
MCFD2Other/UnknownnoEF_hand_dom, EF-hand-dom_pair, EF_Hand_1_Ca_BS
MCFD2-AS1Other/Unknownno

Expression context

Cohort genes with no expression data: 0.

2 cohort genes are a single-cell marker in ≥1 SCXA experiment.

Breadth distribution (Bgee present_calls)

BucketGenes
narrow (1-5 tissues)0
moderate (6-20)0
broad (>20)2
unknown0

Top tissues across cohort

TissueCohort genes
adrenal tissue1
parotid gland1
seminal vesicle1
body of pancreas1
left adrenal gland cortex1
primordial germ cell in gonad1

Per-gene tissue summary (top 30)

SymbolBgee breadthFANTOM5 breadthSCXATop tissues
MCFD2295ubiquitousmarkerparotid gland, seminal vesicle, adrenal tissue
MCFD2-AS1133markerprimordial germ cell in gonad, body of pancreas, left adrenal gland cortex

Protein interactions among cohort

Intra-cohort edges: 0.

Hub genes (top 10 by interactor count)

SymbolInteractor count
MCFD2881
MCFD2-AS10

Structural data

PDB: 1 · AlphaFold-only: 0 · No structure: 1

Cohort genes with PDB structures (top 30)

SymbolUniProtPDB entries
MCFD2Q8NI2217

Function

Pathway analysis

Distinct Reactome pathways touched by cohort: 9. Enrichment computed across 2 evidence-associated genes (1 with Reactome annotation).

Pathways by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 1 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

PathwayCohort genesFoldFDRSample cohort genes
Cargo concentration in the ER1335.9×0.022MCFD2
COPII-mediated vesicle transport1163.1×0.022MCFD2
ER to Golgi Anterograde Transport1132.8×0.022MCFD2
Transport to the Golgi and subsequent modification1102.9×0.022MCFD2
Asparagine N-linked glycosylation160.1×0.030MCFD2
Membrane Trafficking137.1×0.037MCFD2
Vesicle-mediated transport134.8×0.037MCFD2
Post-translational protein modification119.2×0.059MCFD2
Metabolism of proteins112.4×0.081MCFD2

GO biological processes by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 1 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

GO termCohort genesFoldFDRSample cohort genes
vesicle-mediated transport196.3×0.019MCFD2
gene expression179.9×0.019MCFD2
protein transport143.9×0.023MCFD2

Therapeutics

Drug target analysis

Approved (phase 4): 0 · Phase ≥3: 0 · Phased (≥1): 0 · Undrugged: 2

Druggability breadth: 0 of 2 evidence-associated genes (0%) have a ChEMBL target (buckets above are over the deeply-mined display cohort).

Top cohort targets by molecule count

SymbolMoleculesMax phase
MCFD200
MCFD2-AS100

Bioactivity and enzyme data

Enzyme cohort genes (≥1 EC): 0.

Pharmacogenomics

Cohort genes with a PharmGKB record: 1; with CPIC/DPWG dosing guidelines: 0.

No cohort gene has a CPIC/DPWG genotype-guided dosing guideline (PharmGKB).

Chemical tractability of cohort targets

0 approved/phased compounds have measured bioactivity against a cohort gene (and aren’t yet in disease-level trials). This is a research / tractability signal, NOT a therapeutic recommendation — a bioactivity row often reflects off-target or screening binding (e.g. promiscuous kinase inhibitors against a cohort kinase), implying no disease mechanism.

Druggability pyramid

Cohort genes binned by druggability tier (high → low):

TierDefinitionGenesSymbols
AApproved (phase 4 drug)0
BPhased (≥1) drug, not yet approved0
CDruggable family + PDB, no drug0
DDruggable family + AlphaFold only, no drug0
EDifficult family or no structure, no drug2MCFD2, MCFD2-AS1

Undrugged target profiles

2 cohort genes are undrugged. Ranked by ‘starting-point quality’ (assay depth + drugged-partner adjacency).

SymbolChEMBL assaysDrugged partners (top 3)
MCFD20
MCFD2-AS10

Clinical trials & evidence

Clinical trials

Clinical trials: 0.