Hypercalcemia, infantile

disease
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Also known as autosomal recessive hypercalcemia, infantileautosomal recessive infantile hypercalcemiafamilial infantile hypercalcemia with suppressed intact parathyroid hormonehypercalcemia disease of infancyhypercalcemia, idiopathic, of infancyhypercalcemia, infantile, autosomal recessiveidiopathic infantile hypercalcemiainfantile hypercalcemiainfantile hypercalcemia diseaseinfantile onset hypercalcemia disease

Summary

Hypercalcemia, infantile (MONDO:0000212) is a disease with 1 cohort gene and 1 clinical trial. Top therapeutic interventions include rifampin.

At a glance

  • Prevalence: <1 / 1 000 000 (Worldwide) [Orphanet-validated]
  • Cohort genes: 1
  • ClinVar variants: 1
  • Clinical trials: 1

Clinical features

Epidemiology

Prevalence records

2 prevalence record(s), Orphanet:

TypeClassValueGeographyValidation
Cases/families12WorldwideValidated
Point prevalence<1 / 1 000 000WorldwideValidated

Identifiers

Disease identifiers

FieldValue
Canonical namehypercalcemia, infantile
Mondo IDMONDO:0000212
MeSHC562999
OMIM143880
Orphanet300547
NCITC129734
SNOMED CT276645004, 34225008
UMLSC4329374
MedGen1380840
GARD0017374
Is cancer (heuristic)no

Also known as: autosomal recessive hypercalcemia, infantile · autosomal recessive infantile hypercalcemia · familial infantile hypercalcemia with suppressed intact parathyroid hormone · hypercalcemia disease of infancy · hypercalcemia, idiopathic, of infancy · hypercalcemia, infantile · hypercalcemia, infantile, autosomal recessive · idiopathic infantile hypercalcemia · infantile hypercalcemia · infantile hypercalcemia disease · infantile onset hypercalcemia disease

Data availability: 1 ClinVar variant.

Disease family

An umbrella term covering 2 Mondo subtypes.

Classification path: disease › human disease › disease by developmental or physiological process › metabolic diseasemineral metabolism diseasecalcium metabolic diseasehypercalcemia diseasehypercalcemia, infantile

Related subtypes (2): familial hypocalciuric hypercalcemia, humoral hypercalcemia of malignancy

Subtypes (2): hypercalcemia, infantile, 2, hypercalcemia, infantile, 1

Genetics & variants

GWAS landscape

No GWAS associations recorded — common-variant (GWAS) studies don’t cover this disease (typical for Mendelian / rare diseases). See the curated gene cohort and Mendelian overlap below.

Variant details and genetic-evidence tiers

ClinVar germline variants

1 retrieved; paginated sample, class counts are floors:

1 pathogenic/likely pathogenic

ClinVarVariant (HGVS)GeneClassificationReview
929955NM_003052.5(SLC34A1):c.745C>T (p.Arg249Ter)SLC34A1Pathogenic/Likely pathogeniccriteria provided, multiple submitters, no conflicts

Genes & proteins

Mendelian disease overlap and somatic drivers

GenCC: 0 · Orphanet: 4 · OMIM-shared: 0 · Dual-evidence (GWAS+Mendelian): 0

Orphanet rare-disease linkage (cohort genes)

GeneOrphanet IDRare disease
SLC34A1Orphanet:157215Hereditary hypophosphatemic rickets with hypercalciuria
SLC34A1Orphanet:244305Dominant hypophosphatemia with nephrolithiasis or osteoporosis
SLC34A1Orphanet:300547Autosomal recessive infantile hypercalcemia
SLC34A1Orphanet:3337Primary Fanconi renotubular syndrome

Cohort genes → proteins

1 cohort genes, 1 distinct canonical proteins.

Evidence partition

SubsetGenes
multi_evidence1

Cohort genes (full)

SymbolHGNCEnsemblUniProtNameEvidence
SLC34A1HGNC:11019ENSG00000131183Q06495Sodium-dependent phosphate transport protein 2Aclinvar

Cohort function summary

Lead sentence per gene, UniProt-curated.

SymbolProtein nameFunction (lead sentence)
SLC34A1Sodium-dependent phosphate transport protein 2AInvolved in actively transporting phosphate into cells via Na(+) cotransport in the renal brush border membrane.

Protein-family classification

Druggable: 0 · Difficult: 0 · Unknown: 1 · Druggable fraction: 0.0

Family distribution

Cohort families vs a genome-wide background (hypergeometric, BH-FDR; fold = observed/expected). Counts kept; sorted by enrichment, so the catch-all Other/Unknown bucket no longer leads.

FamilyGenesFoldFDR
Other/Unknown11.8×0.558

Per-gene assignment

SymbolFamilyDruggable?ECInterPro (top 3)
SLC34A1Other/UnknownnoNa/Pi_transpt

Expression context

Cohort genes with no expression data: 0.

1 cohort gene are a single-cell marker in ≥1 SCXA experiment.

Breadth distribution (Bgee present_calls)

BucketGenes
narrow (1-5 tissues)0
moderate (6-20)0
broad (>20)1
unknown0

Top tissues across cohort

TissueCohort genes
adult mammalian kidney1
kidney epithelium1
nephron tubule1

Per-gene tissue summary (top 30)

SymbolBgee breadthFANTOM5 breadthSCXATop tissues
SLC34A152tissue_specificmarkernephron tubule, adult mammalian kidney, kidney epithelium

Protein interactions among cohort

Intra-cohort edges: 0.

Hub genes (top 10 by interactor count)

SymbolInteractor count
SLC34A13,362

Structural data

PDB: 0 · AlphaFold-only: 1 · No structure: 0

AlphaFold-only cohort genes (top 30 by pLDDT)

SymbolUniProtpLDDT
SLC34A1Q0649572.24

Function

Pathway analysis

Distinct Reactome pathways touched by cohort: 3. Enrichment computed across 1 evidence-associated genes (1 with Reactome annotation).

Pathways by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 1 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

PathwayCohort genesFoldFDRSample cohort genes
Defective SLC34A1 causes hypophosphatemic nephrolithiasis/osteoporosis 1 (NPHLOP1)15710.0×5e-04SLC34A1
Type II Na+/Pi cotransporters12855.0×5e-04SLC34A1
Surfactant metabolism1368.4×0.003SLC34A1

GO biological processes by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 1 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

GO termCohort genesFoldFDRSample cohort genes
indole metabolic process18426.0×9e-04SLC34A1
gentamycin metabolic process18426.0×9e-04SLC34A1
arsenate ion transmembrane transport18426.0×9e-04SLC34A1
positive regulation of phosphate transmembrane transport18426.0×9e-04SLC34A1
cellular response to phosphate starvation14213.0×0.001SLC34A1
cellular response to metal ion14213.0×0.001SLC34A1
positive regulation of sodium-dependent phosphate transport14213.0×0.001SLC34A1
cellular response to staurosporine13370.4×0.001SLC34A1
positive regulation of membrane potential12808.7×0.001SLC34A1
tricarboxylic acid metabolic process12808.7×0.001SLC34A1
response to mercury ion12407.4×0.001SLC34A1
response to potassium ion12106.5×0.001SLC34A1
response to thyroid hormone12106.5×0.001SLC34A1
dentinogenesis12106.5×0.001SLC34A1
phosphate ion transport11872.4×0.001SLC34A1
sodium-dependent phosphate transport11872.4×0.001SLC34A1
intracellular phosphate ion homeostasis11532.0×0.001SLC34A1
response to magnesium ion11404.3×0.001SLC34A1
cellular response to parathyroid hormone stimulus11404.3×0.001SLC34A1
phosphate ion transmembrane transport11203.7×0.001SLC34A1
glycoprotein metabolic process11123.5×0.001SLC34A1
response to growth hormone11123.5×0.001SLC34A1
response to peptide11123.5×0.001SLC34A1
response to vitamin A11053.2×0.001SLC34A1
phosphate ion homeostasis11053.2×0.001SLC34A1
response to lead ion1936.2×0.001SLC34A1
response to cadmium ion1732.7×0.002SLC34A1
sodium ion import across plasma membrane1624.1×0.002SLC34A1
ossification1227.7×0.005SLC34A1
response to estradiol1198.3×0.005SLC34A1

Therapeutics

Drug target analysis

Approved (phase 4): 1 · Phase ≥3: 1 · Phased (≥1): 1 · Undrugged: 0

Druggability breadth: 1 of 1 evidence-associated genes (100%) have a ChEMBL target (buckets above are over the deeply-mined display cohort).

Genes with an approved drug

The molecule shown is one approved compound that hits the gene — not necessarily a drug of choice or one indicated for this disease.

SymbolExample approved molecule
SLC34A1SODIUM PHOSPHATE, DIBASIC, ANHYDROUS

Top cohort targets by molecule count

SymbolMoleculesMax phase
SLC34A124

Drugs targeting cohort genes (top 30)

MoleculeMax phaseTargets in cohort
SODIUM PHOSPHATE, DIBASIC, ANHYDROUS4SLC34A1
POTASSIUM PHOSPHATE, MONOBASIC4SLC34A1

Bioactivity and enzyme data

Enzyme cohort genes (≥1 EC): 0.

Cohort genes with ChEMBL bioactivity (full, sorted by assay count)

SymbolAssaysType breakdown
SLC34A18Binding:7, Functional:1

Pharmacogenomics

Cohort genes with a PharmGKB record: 1; with CPIC/DPWG dosing guidelines: 0.

No cohort gene has a CPIC/DPWG genotype-guided dosing guideline (PharmGKB).

Chemical tractability of cohort targets

2 approved/phased compounds have measured bioactivity against a cohort gene (and aren’t yet in disease-level trials). This is a research / tractability signal, NOT a therapeutic recommendation — a bioactivity row often reflects off-target or screening binding (e.g. promiscuous kinase inhibitors against a cohort kinase), implying no disease mechanism.

CompoundMax phaseCohort target (bioactivity)
SODIUM PHOSPHATE, DIBASIC, ANHYDROUS4SLC34A1
POTASSIUM PHOSPHATE, MONOBASIC4SLC34A1

Druggability pyramid

Cohort genes binned by druggability tier (high → low):

TierDefinitionGenesSymbols
AApproved (phase 4 drug)1SLC34A1
BPhased (≥1) drug, not yet approved0
CDruggable family + PDB, no drug0
DDruggable family + AlphaFold only, no drug0
EDifficult family or no structure, no drug0

Undrugged target profiles

0 cohort genes are undrugged. Ranked by ‘starting-point quality’ (assay depth + drugged-partner adjacency).

Clinical trials & evidence

Clinical trials

Clinical trials: 1.

Phase distribution (across all retrieved trials)

PhaseTrials
PHASE21

Top trials by phase / activity

NCTPhaseStatusTitle
NCT03301038PHASE2RECRUITINGRifampin in CYP24A1-related Hypercalcemia and Hypercalciuria

Drugs tested across these trials (top 30)

MoleculeMax phaseTrials referencing
RIFAMPIN41