Locked-in syndrome

disease
On this page

Also known as Cerebromedullospinal disconnectionLocked In Syndromelocked-in state

Summary

Locked-in syndrome (MONDO:0016567) is a disease and 16 clinical trials. A subtype of nervous system disorder — broader associated-gene and molecular evidence is on the parent page (see Disease family below).

At a glance

  • Prevalence: <1 / 1 000 000 (Worldwide) [Orphanet-validated]
  • Phenotypes (HPO): 16
  • Clinical trials: 16

Clinical features

Epidemiology

Prevalence records

2 prevalence record(s), Orphanet:

TypeClassValueGeographyValidation
Cases/families33WorldwideValidated
Point prevalence<1 / 1 000 000WorldwideValidated

Signs & symptoms

Clinical features (HPO)

16 HPO clinical features (Orphanet curated; top 16 by frequency):

HPO IDTermFrequency
HP:0000478Abnormality of the eyeVery frequent (80-99%)
HP:0000504Abnormality of visionVery frequent (80-99%)
HP:0000651DiplopiaVery frequent (80-99%)
HP:0000708Atypical behaviorVery frequent (80-99%)
HP:0001257SpasticityVery frequent (80-99%)
HP:0001276HypertoniaVery frequent (80-99%)
HP:0001608Abnormality of the voiceVery frequent (80-99%)
HP:0002093Respiratory insufficiencyVery frequent (80-99%)
HP:0002273TetraparesisVery frequent (80-99%)
HP:0002425AnarthriaVery frequent (80-99%)
HP:0002445TetraplegiaVery frequent (80-99%)
HP:0100021Cerebral palsyVery frequent (80-99%)
HP:0002205Recurrent respiratory infectionsFrequent (30-79%)
HP:0003781Excessive salivationFrequent (30-79%)
HP:0011968Feeding difficultiesFrequent (30-79%)
HP:0000365Hearing impairmentOccasional (5-29%)

Identifiers

Disease identifiers

FieldValue
Canonical namelocked-in syndrome
Mondo IDMONDO:0016567
MeSHD000080422
Orphanet2406
DOIDDOID:12697
ICD-10-CMG83.5
ICD-1117562655
SNOMED CT38023001
UMLSC0023944
MedGen7378
GARD0006919
MedDRA10024792
NORD1376
Is cancer (heuristic)no

Also known as: Cerebromedullospinal disconnection · Locked In Syndrome · locked-in state

Disease family

This is a subtype of nervous system disorder. Genetic, therapeutic, and trial evidence is largely curated at the broader-term level — see the parent page for the associated-gene cohort and molecular evidence.

Classification path: disease › human disease › disease by body system or component › nervous system disorderlocked-in syndrome

Related subtypes (71): congenital nervous system disorder, central nervous system disorder, autoimmune disorder of the nervous system, cranial nerve neuropathy, peripheral nervous system disorder, neuronitis, diplegia of upper limb, retinal disorder, developmental disability, restless legs syndrome, movement disorder, toxic encephalopathy, Barre-Lieou syndrome, Gerstmann syndrome, drug-induced akathisia, drug-induced dyskinesia, stiff-person syndrome, Worster-Drought syndrome, corneal-cerebellar syndrome, pachygyria-intellectual disability-epilepsy syndrome, porencephaly-cerebellar hypoplasia-internal malformations syndrome, symmetrical thalamic calcifications, neonatal brainstem dysfunction, primary orthostatic hypotension, rippling muscle disease with myasthenia gravis, periodic paralysis, qualitative or quantitative protein defects in neuromuscular diseases, specific learning disability, cerebellar hypoplasia-tapetoretinal degeneration syndrome, dopa-responsive dystonia, idiopathic recurrent stupor, chronic lymphocytic inflammation with pontine perivascular enhancement responsive to steroids, spontaneous periodic hypothermia, Sydenham chorea, duplication of the pituitary gland, Balint syndrome, paraneoplastic neurologic syndrome, persistent idiopathic facial pain, serotonin syndrome, hypothalamic adipsic hypernatraemia syndrome, exercise-induced malignant hyperthermia, perineural cyst, neuromuscular disease, neuromyelitis optica, AL amyloidosis, AA amyloidosis, neuroleptic malignant syndrome, infectious disorder of the nervous system, central nervous system malformation, synaptopathy, nervous system neoplasm, sensory ganglionopathy, radiculitis, wet beriberi, perceptual disorders, prepubertal anorexia nervosa, neurocutaneous syndrome, neurovascular disorder, Wallerian degeneration, nervous system injury, neurosarcoidosis, neuroendocrine disorder, tubulinopathy, atactic disorder, hereditary neurological disease, meningitis-retention syndrome, KIF1A related neurological disorder, neurological pain disorder, neurodevelopmental disorder, post 5-alpha-reductase inhibitors treatment syndrome, post-selective serotonin reuptake inhibitor sexual dysfunction

Genetics & variants

GWAS landscape

No GWAS associations recorded — common-variant (GWAS) studies don’t cover this disease (typical for Mendelian / rare diseases). See the curated gene cohort and Mendelian overlap below.

Variant details and genetic-evidence tiers

No tiered GWAS variants or ClinVar records for this disease.

Genes & proteins

No associated-gene cohort resolved for this disease. Atlas builds the molecular and therapeutic sections — associated genes, protein families, druggability, pathways, interactions, and drug associations — by aggregating over a disease’s associated genes (resolved via GWAS / GenCC / ClinVar / CIViC), and none resolved here. This is expected for antibody-mediated, autoimmune, or otherwise non-gene-defined conditions; the curated evidence for this disease is its clinical features, GWAS susceptibility, and clinical trials (above).

Function

No pathway enrichment — requires an associated-gene cohort.

Therapeutics

No druggable-target or therapeutic data for this disease’s cohort.

Clinical trials & evidence

Clinical trials

Clinical trials: 16.

Phase distribution (across all retrieved trials)

PhaseTrials
Not specified16

Top trials by phase / activity

NCTPhaseStatusTitle
NCT00912041Not specifiedRECRUITINGBrainGate2: Feasibility Study of an Intracortical Neural Interface System for Persons With Tetraplegia
NCT03567213Not specifiedRECRUITINGInvestigation on the Cortical Communication (CortiCom) System
NCT05470478Not specifiedNOT_YET_RECRUITINGiBCI Optimization for Veterans With Paralysis
NCT05724173Not specifiedRECRUITINGFeasibility of the BrainGate2 Neural Interface System in Persons With Tetraplegia
NCT06094205Not specifiedRECRUITINGFeasibility of the BrainGate2 Neural Interface System in Persons With Tetraplegia (BG-Speech-02)
NCT06207591Not specifiedRECRUITINGInvestigation on the Cortical Communication System
NCT07257601Not specifiedNOT_YET_RECRUITINGTDCS-RTMS Intervention for Motor Function
NCT07460037Not specifiedRECRUITINGChinese-Specific Speech Imagery Coding Using High-Density ECoG
NCT01964664Not specifiedCOMPLETEDMindfulness Meditation for Subjects With Severe Speech and Physical Impairments
NCT02224469Not specifiedCOMPLETEDFirst Study With a Brain Implant to Help Locked-in Patients Communicate at Home
NCT02772302Not specifiedCOMPLETEDFeasibility of mindBEAGLE in Disorders of Consciousness or Locked-In Syndrome
NCT03213561Not specifiedTERMINATEDStable and Independent Communication Brain-computer Interfaces
NCT03811301Not specifiedUNKNOWN[BrainConnexion] - Neurodevice Phase I Trial
NCT04468919Not specifiedCOMPLETEDOptimizing BCI-FIT: Brain Computer Interface - Functional Implementation Toolkit
NCT04576650Not specifiedWITHDRAWNBrain-Computer Interface Implant for Severe Communication Disability
NCT05444075Not specifiedUNKNOWNA Method for Communication With Arabic Patients Suffering From Classic Locked- in Syndrome

No linked Atlas pages yet — the cross-entity mesh grows as the corpus expands.