mitochondrial DNA depletion syndrome 9

disease
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Also known as lactic acidosis congenital infantilelactic acidosis, fatal infantilemitochondrial DNA depletion syndrome 9 (encephalomyopathic type with methylmalonic aciduria)mitochondrial DNA depletion syndrome caused by mutation in SUCLG1mitochondrial DNA depletion syndrome type 9MTDPS9succinate-CoA ligase deficiencySUCLG1 mitochondrial DNA depletion syndrome

Summary

mitochondrial DNA depletion syndrome 9 (MONDO:0009504) is a disease caused by SUCLG1 (GenCC Definitive), with 2 cohort genes.

At a glance

  • Prevalence: Unknown (Worldwide)
  • Causal gene: SUCLG1 (GenCC Definitive)
  • Cohort genes: 2
  • ClinVar variants: 288
  • Phenotypes (HPO): 64

Clinical features

Signs & symptoms

Clinical features (HPO)

64 HPO clinical features (Orphanet curated; top 50 by frequency):

HPO IDTermFrequency
HP:0002912Methylmalonic acidemiaObligate (100%)
HP:0012120Methylmalonic aciduriaObligate (100%)
HP:0001263Global developmental delayVery frequent (80-99%)
HP:00035353-Methylglutaconic aciduriaVery frequent (80-99%)
HP:0008947Floppy infantVery frequent (80-99%)
HP:0012379Abnormal enzyme/coenzyme activityVery frequent (80-99%)
HP:0012751Abnormal basal ganglia MRI signal intensityVery frequent (80-99%)
HP:0001249Intellectual disabilityFrequent (30-79%)
HP:0001298EncephalopathyFrequent (30-79%)
HP:0001397Hepatic steatosisFrequent (30-79%)
HP:0001508Failure to thriveFrequent (30-79%)
HP:0001510Growth delayFrequent (30-79%)
HP:0002059Cerebral atrophyFrequent (30-79%)
HP:0002151Increased circulating lactate concentrationFrequent (30-79%)
HP:0002240HepatomegalyFrequent (30-79%)
HP:0002490Increased CSF lactateFrequent (30-79%)
HP:0002910Elevated circulating hepatic transaminase concentrationFrequent (30-79%)
HP:0003128Lactic acidosisFrequent (30-79%)
HP:0003202Skeletal muscle atrophyFrequent (30-79%)
HP:0008347Decreased activity of mitochondrial complex IVFrequent (30-79%)
HP:0011923Decreased activity of mitochondrial complex IFrequent (30-79%)
HP:0011924Decreased activity of mitochondrial complex IIIFrequent (30-79%)
HP:0011968Feeding difficultiesFrequent (30-79%)
HP:0000252MicrocephalyOccasional (5-29%)
HP:0000407Sensorineural hearing impairmentOccasional (5-29%)
HP:0000486StrabismusOccasional (5-29%)
HP:0000508PtosisOccasional (5-29%)
HP:0000718Aggressive behaviorOccasional (5-29%)
HP:0000736Short attention spanOccasional (5-29%)
HP:0000975HyperhidrosisOccasional (5-29%)
HP:0001250SeizureOccasional (5-29%)
HP:0001266ChoreoathetosisOccasional (5-29%)
HP:0001276HypertoniaOccasional (5-29%)
HP:0001332DystoniaOccasional (5-29%)
HP:0001336MyoclonusOccasional (5-29%)
HP:0001371Flexion contractureOccasional (5-29%)
HP:0001639Hypertrophic cardiomyopathyOccasional (5-29%)
HP:0001943HypoglycemiaOccasional (5-29%)
HP:0002013VomitingOccasional (5-29%)
HP:0002020Gastroesophageal refluxOccasional (5-29%)
HP:0002045HypothermiaOccasional (5-29%)
HP:0002098Respiratory distressOccasional (5-29%)
HP:0002104ApneaOccasional (5-29%)
HP:0002205Recurrent respiratory infectionsOccasional (5-29%)
HP:0002317Unsteady gaitOccasional (5-29%)
HP:0002352LeukoencephalopathyOccasional (5-29%)
HP:0002360Sleep abnormalityOccasional (5-29%)
HP:0002487Hyperkinetic movementsOccasional (5-29%)
HP:0003200Ragged-red muscle fibersOccasional (5-29%)
HP:0003201RhabdomyolysisOccasional (5-29%)

Identifiers

Disease identifiers

FieldValue
Canonical namemitochondrial DNA depletion syndrome 9
Mondo IDMONDO:0009504
MeSHC538134, C566885
OMIM245400
Orphanet17
DOIDDOID:0080128
SNOMED CT715338007
UMLSC3151476
MedGen462826
GARD0003163
Is cancer (heuristic)no

Also known as: lactic acidosis congenital infantile · lactic acidosis, fatal infantile · mitochondrial DNA depletion syndrome 9 · mitochondrial DNA depletion syndrome 9 (encephalomyopathic type with methylmalonic aciduria) · mitochondrial DNA depletion syndrome caused by mutation in SUCLG1 · mitochondrial DNA depletion syndrome type 9 · MTDPS9 · succinate-CoA ligase deficiency · SUCLG1 mitochondrial DNA depletion syndrome

Data availability: 288 ClinVar variants · 4 GenCC gene-disease records · 1 cell line.

Disease family

Classification path: disease › human disease › disease by developmental or physiological process › metabolic diseaselactic acidosismitochondrial DNA depletion syndrome 9

Related subtypes (2): cardiomyopathy-hypotonia-lactic acidosis syndrome, acquired lactic acidosis

Genetics & variants

GWAS landscape

No GWAS associations recorded — common-variant (GWAS) studies don’t cover this disease (typical for Mendelian / rare diseases). See the curated gene cohort and Mendelian overlap below.

Variant details and genetic-evidence tiers

ClinVar germline variants

288 retrieved; paginated sample, class counts are floors:

125 likely benign, 99 uncertain significance, 24 pathogenic, 19 conflicting classifications of pathogenicity, 8 likely pathogenic, 7 benign/likely benign, 6 benign

ClinVarVariant (HGVS)GeneClassificationReview
998016NM_003849.4(SUCLG1):c.[460C>T;987dup]Pathogenicno assertion criteria provided
1012244NM_003849.4(SUCLG1):c.460C>T (p.Arg154Ter)SUCLG1Pathogeniccriteria provided, single submitter
1071175NC_000002.11:g.(?84650850)(84686413_?)delSUCLG1Pathogeniccriteria provided, single submitter
1185061NM_003849.4(SUCLG1):c.724del (p.Ile242fs)SUCLG1Pathogenicno assertion criteria provided
1325153NM_003849.4(SUCLG1):c.814C>T (p.Gln272Ter)SUCLG1Pathogeniccriteria provided, single submitter
1375896NM_003849.4(SUCLG1):c.169_170del (p.Lys57fs)SUCLG1Pathogeniccriteria provided, single submitter
1686238NM_003849.4(SUCLG1):c.643C>T (p.Gln215Ter)SUCLG1Pathogeniccriteria provided, single submitter
1686239NM_003849.4(SUCLG1):c.458T>A (p.Val153Glu)SUCLG1Pathogeniccriteria provided, single submitter
18409NM_003849.4(SUCLG1):c.254G>C (p.Gly85Ala)SUCLG1Pathogenicno assertion criteria provided
18410NM_003849.4(SUCLG1):c.509C>G (p.Pro170Arg)SUCLG1Pathogenicno assertion criteria provided
18411NM_003849.4(SUCLG1):c.97+3G>CSUCLG1Pathogenicno assertion criteria provided
18412NM_003849.4(SUCLG1):c.448C>T (p.Gln150Ter)SUCLG1Pathogenicno assertion criteria provided
212328NM_003849.4(SUCLG1):c.507del (p.Asn171fs)SUCLG1Pathogeniccriteria provided, single submitter
2982185NM_003849.4(SUCLG1):c.445C>T (p.Gln149Ter)SUCLG1Pathogeniccriteria provided, single submitter
3005619NM_003849.4(SUCLG1):c.835del (p.Ser279fs)SUCLG1Pathogeniccriteria provided, single submitter
3651171NM_003849.4(SUCLG1):c.583_586del (p.Arg195fs)SUCLG1Pathogeniccriteria provided, single submitter
3724793NM_003849.4(SUCLG1):c.199C>T (p.Gln67Ter)SUCLG1Pathogeniccriteria provided, single submitter
4688454NM_003849.4(SUCLG1):c.937G>T (p.Glu313Ter)SUCLG1Pathogeniccriteria provided, single submitter
4712015NM_003849.4(SUCLG1):c.390_393del (p.Asn130fs)SUCLG1Pathogeniccriteria provided, single submitter
4721624NM_003849.4(SUCLG1):c.220C>T (p.Gln74Ter)SUCLG1Pathogeniccriteria provided, single submitter
632365NM_003849.4(SUCLG1):c.152_153del (p.Tyr51fs)SUCLG1Pathogenicno assertion criteria provided
801730NM_003849.4(SUCLG1):c.201+1G>TSUCLG1Pathogeniccriteria provided, single submitter
818207NM_003849.4(SUCLG1):c.457_458delinsTA (p.Val153Ter)SUCLG1Pathogeniccriteria provided, single submitter
992828NM_003849.4(SUCLG1):c.626C>A (p.Ala209Glu)SUCLG1Pathogeniccriteria provided, multiple submitters, no conflicts
2130397NM_003849.4(SUCLG1):c.826-1G>ASUCLG1Likely pathogeniccriteria provided, single submitter
2434026NM_003849.4(SUCLG1):c.790G>T (p.Glu264Ter)SUCLG1Likely pathogeniccriteria provided, single submitter
2734239NM_003849.4(SUCLG1):c.319-1G>ASUCLG1Likely pathogeniccriteria provided, single submitter
2850714NM_003849.4(SUCLG1):c.673+1G>CSUCLG1Likely pathogeniccriteria provided, single submitter
3247379NC_000002.11:g.(?84650870)(84652747_?)delSUCLG1Likely pathogeniccriteria provided, single submitter
3780681NM_003849.4(SUCLG1):c.787G>A (p.Glu263Lys)SUCLG1Likely pathogeniccriteria provided, single submitter

Genes & proteins

Mendelian disease overlap and somatic drivers

GenCC: 5 · Orphanet: 1 · OMIM-shared: 0 · Dual-evidence (GWAS+Mendelian): 0

GenCC gene–disease validity (cohort genes)

the Disease column is the GenCC-asserted condition — a cohort gene’s strongest validity may be for a related predisposition syndrome.

GeneClassificationInheritanceDiseaseRecords
SUCLG1DefinitiveAutosomal recessivemitochondrial DNA depletion syndrome 95

Orphanet rare-disease linkage (cohort genes)

GeneOrphanet IDRare disease
SUCLG1Orphanet:17Fatal infantile lactic acidosis with methylmalonic aciduria

Cohort genes → proteins

2 cohort genes, 2 distinct canonical proteins.

Evidence partition

SubsetGenes
multi_evidence2

Cohort genes (full)

SymbolHGNCEnsemblUniProtNameEvidence
SUCLG1HGNC:11449ENSG00000163541P53597Succinate–CoA ligase [ADP/GDP-forming] subunit alpha, mitochondrialgencc,clinvar
SUCLG2HGNC:11450ENSG00000172340Q96I99Succinate–CoA ligase [GDP-forming] subunit beta, mitochondrialclinvar

Cohort function summary

Lead sentence per gene, UniProt-curated.

SymbolProtein nameFunction (lead sentence)
SUCLG1Succinate–CoA ligase [ADP/GDP-forming] subunit alpha, mitochondrialSuccinyl-CoA synthetase functions in the citric acid cycle (TCA), coupling the hydrolysis of succinyl-CoA to the synthesis of either ATP or GTP and thus represents the only step of substrate-level phosphorylation in the TCA.
SUCLG2Succinate–CoA ligase [GDP-forming] subunit beta, mitochondrialGTP-specific succinyl-CoA synthetase functions in the citric acid cycle (TCA), coupling the hydrolysis of succinyl-CoA to the synthesis of GTP and thus represents the only step of substrate-level phosphorylation in the TCA.

Protein-family classification

Druggable: 2 · Difficult: 0 · Unknown: 0 · Druggable fraction: 1.0

Family distribution

Cohort families vs a genome-wide background (hypergeometric, BH-FDR; fold = observed/expected). Counts kept; sorted by enrichment, so the catch-all Other/Unknown bucket no longer leads.

FamilyGenesFoldFDR
Enzyme (other)212.0×0.007

Per-gene assignment

SymbolFamilyDruggable?ECInterPro (top 3)
SUCLG1Enzyme (other)yes6.2.1.4CoA-bd, CoA_lig_alpha, SUCC_ACL_C
SUCLG2Enzyme (other)yes6.2.1.4Succ_CoA_ligase-like_bsu, SUCC_ACL_C, ATP-grasp_succ-CoA_synth-type

Expression context

Cohort genes with no expression data: 0.

2 cohort genes are a single-cell marker in ≥1 SCXA experiment.

Breadth distribution (Bgee present_calls)

BucketGenes
narrow (1-5 tissues)0
moderate (6-20)0
broad (>20)2
unknown0

Top tissues across cohort

TissueCohort genes
metanephric glomerulus1
nephron tubule1
renal glomerulus1
colonic mucosa1
mucosa of sigmoid colon1
rectum1

Per-gene tissue summary (top 30)

SymbolBgee breadthFANTOM5 breadthSCXATop tissues
SUCLG1288ubiquitousmarkernephron tubule, renal glomerulus, metanephric glomerulus
SUCLG2286ubiquitousmarkercolonic mucosa, mucosa of sigmoid colon, rectum

Protein interactions among cohort

Intra-cohort edges: 1.

Hub genes (top 10 by interactor count)

SymbolInteractor count
SUCLG26,231
SUCLG13,794

Intra-cohort edges

ABSources
SUCLG1SUCLG2biogrid_interaction, intact, string_interaction

Structural data

PDB: 2 · AlphaFold-only: 0 · No structure: 0

Cohort genes with PDB structures (top 30)

SymbolUniProtPDB entries
SUCLG1P535978
SUCLG2Q96I996

Function

Pathway analysis

Distinct Reactome pathways touched by cohort: 5. Enrichment computed across 2 evidence-associated genes (2 with Reactome annotation).

Pathways by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 2 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

PathwayCohort genesFoldFDRSample cohort genes
Citric acid cycle (TCA cycle)2423.0×3e-05SUCLG1, SUCLG2
Aerobic respiration and respiratory electron transport288.5×3e-04SUCLG1, SUCLG2
Metabolism211.6×0.012SUCLG1, SUCLG2
Mitochondrial protein degradation157.1×0.022SUCLG2
Metabolism of proteins16.2×0.155SUCLG2

GO biological processes by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 2 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

GO termCohort genesFoldFDRSample cohort genes
succinyl-CoA catabolic process22407.4×6e-07SUCLG1, SUCLG2
tricarboxylic acid cycle2510.7×7e-06SUCLG1, SUCLG2
succinyl-CoA metabolic process11685.2×6e-04SUCLG2
succinate metabolic process11685.2×6e-04SUCLG2

Therapeutics

Drug target analysis

Approved (phase 4): 0 · Phase ≥3: 0 · Phased (≥1): 0 · Undrugged: 2

Druggability breadth: 2 of 2 evidence-associated genes (100%) have a ChEMBL target (buckets above are over the deeply-mined display cohort).

Top cohort targets by molecule count

SymbolMoleculesMax phase
SUCLG100
SUCLG200

Bioactivity and enzyme data

Enzyme cohort genes (≥1 EC): 2.

Cohort genes with ChEMBL bioactivity (full, sorted by assay count)

SymbolAssaysType breakdown
SUCLG11Binding:1
SUCLG21Binding:1

Cohort enzymes (BRENDA EC)

SymbolEC numbersNames
SUCLG16.2.1.4, 6.2.1.5succinate-CoA ligase (GDP-forming), succinate-CoA ligase (ADP-forming)
SUCLG26.2.1.4succinate-CoA ligase (GDP-forming)

Pharmacogenomics

Cohort genes with a PharmGKB record: 2; with CPIC/DPWG dosing guidelines: 0.

No cohort gene has a CPIC/DPWG genotype-guided dosing guideline (PharmGKB).

Chemical tractability of cohort targets

0 approved/phased compounds have measured bioactivity against a cohort gene (and aren’t yet in disease-level trials). This is a research / tractability signal, NOT a therapeutic recommendation — a bioactivity row often reflects off-target or screening binding (e.g. promiscuous kinase inhibitors against a cohort kinase), implying no disease mechanism.

Druggability pyramid

Cohort genes binned by druggability tier (high → low):

TierDefinitionGenesSymbols
AApproved (phase 4 drug)0
BPhased (≥1) drug, not yet approved0
CDruggable family + PDB, no drug2SUCLG1, SUCLG2
DDruggable family + AlphaFold only, no drug0
EDifficult family or no structure, no drug0

Undrugged target profiles

2 cohort genes are undrugged. Ranked by ‘starting-point quality’ (assay depth + drugged-partner adjacency).

SymbolChEMBL assaysDrugged partners (top 3)
SUCLG11
SUCLG21

Clinical trials & evidence

Clinical trials

Clinical trials: 0.