Non-acquired combined pituitary hormone deficiency

disease
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Also known as congenital combined pituitary hormone deficiencycongenital hypopituitarism

Summary

Non-acquired combined pituitary hormone deficiency (MONDO:0018762) is a disease (an umbrella term covering 7 Mondo subtypes) with 1 cohort gene and 1 clinical trial.

At a glance

  • Prevalence: 1-5 / 10 000 (Europe) [Orphanet-validated]
  • Umbrella term: 7 Mondo subtypes
  • Cohort genes: 1
  • ClinVar variants: 1
  • Clinical trials: 1

Clinical features

Epidemiology

Prevalence records

2 prevalence record(s), Orphanet:

TypeClassValueGeographyValidation
Point prevalence1-5 / 10 000EuropeValidated
Prevalence at birth1-5 / 10 00029EuropeValidated

Identifiers

Disease identifiers

FieldValue
Canonical namenon-acquired combined pituitary hormone deficiency
Mondo IDMONDO:0018762
Orphanet467
UMLSC5680091
MedGen1842250
GARD0002252
Is cancer (heuristic)no

Also known as: congenital combined pituitary hormone deficiency · congenital hypopituitarism

Data availability: 1 ClinVar variant.

Disease family

An umbrella term covering 7 Mondo subtypes.

Classification path: disease › human disease › disease by body system or component › endocrine system disorder › pituitary deficiency › non-acquired pituitary hormone deficiency › non-acquired combined pituitary hormone deficiency

Related subtypes (4): isolated thyroid-stimulating hormone deficiency, short stature due to GHSR deficiency, congenital hypogonadotropic hypogonadism, pituitary stalk interruption syndrome

Subtypes (7): Pallister-Hall syndrome, non-acquired combined pituitary hormone deficiency with spine abnormalities, short stature-pituitary and cerebellar defects-small sella turcica syndrome, ANE syndrome, postaxial polydactyly-anterior pituitary anomalies-facial dysmorphism syndrome, holoprosencephaly, deficiency in anterior pituitary function - variable immunodeficiency syndrome

Genetics & variants

GWAS landscape

No GWAS associations recorded — common-variant (GWAS) studies don’t cover this disease (typical for Mendelian / rare diseases). See the curated gene cohort and Mendelian overlap below.

Variant details and genetic-evidence tiers

ClinVar germline variants

1 retrieved; paginated sample, class counts are floors:

1 likely pathogenic

ClinVarVariant (HGVS)GeneClassificationReview
3544360NM_021784.5(FOXA2):c.619C>T (p.Gln207Ter)FOXA2Likely pathogeniccriteria provided, single submitter

Genes & proteins

Mendelian disease overlap and somatic drivers

GenCC: 0 · Orphanet: 1 · OMIM-shared: 0 · Dual-evidence (GWAS+Mendelian): 0

Orphanet rare-disease linkage (cohort genes)

GeneOrphanet IDRare disease
FOXA2Orphanet:95494Combined pituitary hormone deficiencies, genetic forms

Cohort genes → proteins

1 cohort genes, 1 distinct canonical proteins.

Evidence partition

SubsetGenes
multi_evidence1

Cohort genes (full)

SymbolHGNCEnsemblUniProtNameEvidence
FOXA2HGNC:5022ENSG00000125798Q9Y261Hepatocyte nuclear factor 3-betaclinvar

Cohort function summary

Lead sentence per gene, UniProt-curated.

SymbolProtein nameFunction (lead sentence)
FOXA2Hepatocyte nuclear factor 3-betaTranscription factor that is involved in embryonic development, establishment of tissue-specific gene expression and regulation of gene expression in differentiated tissues.

Protein-family classification

Druggable: 0 · Difficult: 1 · Unknown: 0 · Druggable fraction: 0.0

Family distribution

Cohort families vs a genome-wide background (hypergeometric, BH-FDR; fold = observed/expected). Counts kept; sorted by enrichment, so the catch-all Other/Unknown bucket no longer leads.

FamilyGenesFoldFDR
Transcription factor18.3×0.121

Per-gene assignment

SymbolFamilyDruggable?ECInterPro (top 3)
FOXA2Transcription factornoFork_head_dom, Fork-head_N, TF_fork_head_CS_1

Expression context

Cohort genes with no expression data: 0.

1 cohort gene are a single-cell marker in ≥1 SCXA experiment.

Breadth distribution (Bgee present_calls)

BucketGenes
narrow (1-5 tissues)0
moderate (6-20)0
broad (>20)1
unknown0

Top tissues across cohort

TissueCohort genes
buccal mucosa cell1
pancreatic ductal cell1
pylorus1

Per-gene tissue summary (top 30)

SymbolBgee breadthFANTOM5 breadthSCXATop tissues
FOXA2105broadmarkerpancreatic ductal cell, pylorus, buccal mucosa cell

Protein interactions among cohort

Intra-cohort edges: 0.

Hub genes (top 10 by interactor count)

SymbolInteractor count
FOXA22,789

Structural data

PDB: 1 · AlphaFold-only: 0 · No structure: 0

Cohort genes with PDB structures (top 30)

SymbolUniProtPDB entries
FOXA2Q9Y2613

Function

Pathway analysis

Distinct Reactome pathways touched by cohort: 7. Enrichment computed across 1 evidence-associated genes (1 with Reactome annotation).

Pathways by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 1 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

PathwayCohort genesFoldFDRSample cohort genes
Positive Regulation of CDH1 Gene Transcription1951.7×0.003FOXA2
Formation of axial mesoderm1815.7×0.003FOXA2
Formation of definitive endoderm1713.8×0.003FOXA2
Developmental Lineage of Multipotent Pancreatic Progenitor Cells1601.0×0.003FOXA2
Regulation of gene expression in beta cells1519.1×0.003FOXA2
Developmental Lineage of Pancreatic Acinar Cells1300.5×0.004FOXA2
Developmental Lineage of Pancreatic Ductal Cells1228.4×0.004FOXA2

GO biological processes by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 1 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

GO termCohort genesFoldFDRSample cohort genes
response to interleukin-614213.0×0.003FOXA2
positive regulation of gastrulation12407.4×0.003FOXA2
regulation of blood coagulation11872.4×0.003FOXA2
primitive streak formation11404.3×0.003FOXA2
positive regulation of cell-cell adhesion mediated by cadherin11296.3×0.003FOXA2
positive regulation of embryonic development11123.5×0.003FOXA2
endocrine pancreas development1936.2×0.003FOXA2
regulation of insulin secretion involved in cellular response to glucose stimulus1936.2×0.003FOXA2
dopaminergic neuron differentiation1624.1×0.003FOXA2
cell fate specification1526.6×0.004FOXA2
negative regulation of epithelial to mesenchymal transition1411.0×0.004FOXA2
adult locomotory behavior1300.9×0.005FOXA2
anatomical structure morphogenesis1139.3×0.010FOXA2
chromatin organization199.1×0.014FOXA2
cell differentiation129.1×0.042FOXA2
positive regulation of DNA-templated transcription127.9×0.042FOXA2
negative regulation of transcription by RNA polymerase II117.7×0.063FOXA2
positive regulation of transcription by RNA polymerase II114.9×0.071FOXA2
regulation of transcription by RNA polymerase II111.7×0.086FOXA2

Therapeutics

Drug target analysis

Approved (phase 4): 0 · Phase ≥3: 0 · Phased (≥1): 0 · Undrugged: 1

Druggability breadth: 0 of 1 evidence-associated genes (0%) have a ChEMBL target (buckets above are over the deeply-mined display cohort).

Top cohort targets by molecule count

SymbolMoleculesMax phase
FOXA200

Bioactivity and enzyme data

Enzyme cohort genes (≥1 EC): 0.

Pharmacogenomics

Cohort genes with a PharmGKB record: 1; with CPIC/DPWG dosing guidelines: 0.

No cohort gene has a CPIC/DPWG genotype-guided dosing guideline (PharmGKB).

Chemical tractability of cohort targets

0 approved/phased compounds have measured bioactivity against a cohort gene (and aren’t yet in disease-level trials). This is a research / tractability signal, NOT a therapeutic recommendation — a bioactivity row often reflects off-target or screening binding (e.g. promiscuous kinase inhibitors against a cohort kinase), implying no disease mechanism.

Druggability pyramid

Cohort genes binned by druggability tier (high → low):

TierDefinitionGenesSymbols
AApproved (phase 4 drug)0
BPhased (≥1) drug, not yet approved0
CDruggable family + PDB, no drug0
DDruggable family + AlphaFold only, no drug0
EDifficult family or no structure, no drug1FOXA2

Undrugged target profiles

1 cohort genes are undrugged. Ranked by ‘starting-point quality’ (assay depth + drugged-partner adjacency).

SymbolChEMBL assaysDrugged partners (top 3)
FOXA20

Clinical trials & evidence

Clinical trials

Clinical trials: 1.

Phase distribution (across all retrieved trials)

PhaseTrials
Not specified1

Top trials by phase / activity

NCTPhaseStatusTitle
NCT04463316Not specifiedRECRUITINGGROWing Up With Rare GENEtic Syndromes