obesity due to CEP19 deficiency

disease
On this page

Also known as morbid obesity and spermatogenic failureMOSPGF

Summary

obesity due to CEP19 deficiency (MONDO:0014309) is a disease caused by CEP19 (GenCC Strong), with 1 cohort gene.

At a glance

  • Prevalence: <1 / 1 000 000 (Worldwide) [Orphanet-validated]
  • Causal gene: CEP19 (GenCC Strong)
  • Cohort genes: 1
  • ClinVar variants: 3

Clinical features

Epidemiology

Prevalence records

2 prevalence record(s), Orphanet:

TypeClassValueGeographyValidation
Cases/families15WorldwideValidated
Point prevalence<1 / 1 000 000WorldwideValidated

Identifiers

Disease identifiers

FieldValue
Canonical nameobesity due to CEP19 deficiency
Mondo IDMONDO:0014309
OMIM615703
Orphanet397615
UMLSC3810324
MedGen816654
GARD0017631
Is cancer (heuristic)no

Also known as: morbid obesity and spermatogenic failure · MOSPGF

Data availability: 3 ClinVar variants · 4 GenCC gene-disease records.

Disease family

Classification path: disease › human disease › disease by etiologic mechanism › disease of genetic or genomic mechanism › hereditary diseaseinherited obesityobesity due to CEP19 deficiency

Related subtypes (6): obesity due to prohormone convertase I deficiency, obesity due to pro-opiomelanocortin deficiency, obesity due to congenital leptin deficiency, obesity due to leptin receptor gene deficiency, obesity due to SIM1 deficiency, obesity due to melanocortin 4 receptor deficiency

Genetics & variants

GWAS landscape

No GWAS associations recorded — common-variant (GWAS) studies don’t cover this disease (typical for Mendelian / rare diseases). See the curated gene cohort and Mendelian overlap below.

Variant details and genetic-evidence tiers

ClinVar germline variants

3 retrieved; paginated sample, class counts are floors:

1 conflicting classifications of pathogenicity, 1 uncertain significance, 1 benign

ClinVarVariant (HGVS)GeneClassificationReview
120189NM_032898.5(CEP19):c.232C>T (p.Arg78Ter)CEP19Conflicting classifications of pathogenicitycriteria provided, conflicting classifications
1384958NM_032898.5(CEP19):c.283C>T (p.Arg95Trp)CEP19Uncertain significancecriteria provided, multiple submitters, no conflicts
761411NM_032898.5(CEP19):c.-11T>CCEP19Benigncriteria provided, multiple submitters, no conflicts

Genes & proteins

Mendelian disease overlap and somatic drivers

GenCC: 5 · Orphanet: 2 · OMIM-shared: 0 · Dual-evidence (GWAS+Mendelian): 0

GenCC gene–disease validity (cohort genes)

the Disease column is the GenCC-asserted condition — a cohort gene’s strongest validity may be for a related predisposition syndrome.

GeneClassificationInheritanceDiseaseRecords
CEP19StrongAutosomal recessiveobesity due to CEP19 deficiency5

Orphanet rare-disease linkage (cohort genes)

GeneOrphanet IDRare disease
CEP19Orphanet:110Bardet-Biedl syndrome
CEP19Orphanet:397615Obesity due to CEP19 deficiency

Cohort genes → proteins

1 cohort genes, 1 distinct canonical proteins.

Evidence partition

SubsetGenes
multi_evidence1

Cohort genes (full)

SymbolHGNCEnsemblUniProtNameEvidence
CEP19HGNC:28209ENSG00000174007Q96LK0Centrosomal protein of 19 kDagencc,clinvar

Cohort function summary

Lead sentence per gene, UniProt-curated.

SymbolProtein nameFunction (lead sentence)
CEP19Centrosomal protein of 19 kDaRequired for ciliation.

Protein-family classification

Druggable: 0 · Difficult: 0 · Unknown: 1 · Druggable fraction: 0.0

Family distribution

Cohort families vs a genome-wide background (hypergeometric, BH-FDR; fold = observed/expected). Counts kept; sorted by enrichment, so the catch-all Other/Unknown bucket no longer leads.

FamilyGenesFoldFDR
Other/Unknown11.8×0.558

Per-gene assignment

SymbolFamilyDruggable?ECInterPro (top 3)
CEP19Other/UnknownnoCEP19

Expression context

Cohort genes with no expression data: 0.

Breadth distribution (Bgee present_calls)

BucketGenes
narrow (1-5 tissues)0
moderate (6-20)0
broad (>20)1
unknown0

Top tissues across cohort

TissueCohort genes
blood1
male germ line stem cell (sensu Vertebrata) in testis1
primordial germ cell in gonad1

Per-gene tissue summary (top 30)

SymbolBgee breadthFANTOM5 breadthSCXATop tissues
CEP19214ubiquitousyesmale germ line stem cell (sensu Vertebrata) in testis, primordial germ cell in gonad, blood

Protein interactions among cohort

Intra-cohort edges: 0.

Hub genes (top 10 by interactor count)

SymbolInteractor count
CEP191,037

Structural data

PDB: 0 · AlphaFold-only: 1 · No structure: 0

AlphaFold-only cohort genes (top 30 by pLDDT)

SymbolUniProtpLDDT
CEP19Q96LK082.85

Function

Pathway analysis

Distinct Reactome pathways touched by cohort: 0. Enrichment computed across 1 evidence-associated genes (0 with Reactome annotation).

GO biological processes by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 1 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

GO termCohort genesFoldFDRSample cohort genes
trans-Golgi to periciliary membrane compartment transport116852.0×2e-04CEP19
microtubule anchoring at centrosome11404.3×0.001CEP19
cilium assembly173.6×0.014CEP19

Therapeutics

Drug target analysis

Approved (phase 4): 0 · Phase ≥3: 0 · Phased (≥1): 0 · Undrugged: 1

Druggability breadth: 0 of 1 evidence-associated genes (0%) have a ChEMBL target (buckets above are over the deeply-mined display cohort).

Top cohort targets by molecule count

SymbolMoleculesMax phase
CEP1900

Bioactivity and enzyme data

Enzyme cohort genes (≥1 EC): 0.

Pharmacogenomics

Cohort genes with a PharmGKB record: 1; with CPIC/DPWG dosing guidelines: 0.

No cohort gene has a CPIC/DPWG genotype-guided dosing guideline (PharmGKB).

Chemical tractability of cohort targets

0 approved/phased compounds have measured bioactivity against a cohort gene (and aren’t yet in disease-level trials). This is a research / tractability signal, NOT a therapeutic recommendation — a bioactivity row often reflects off-target or screening binding (e.g. promiscuous kinase inhibitors against a cohort kinase), implying no disease mechanism.

Druggability pyramid

Cohort genes binned by druggability tier (high → low):

TierDefinitionGenesSymbols
AApproved (phase 4 drug)0
BPhased (≥1) drug, not yet approved0
CDruggable family + PDB, no drug0
DDruggable family + AlphaFold only, no drug0
EDifficult family or no structure, no drug1CEP19

Undrugged target profiles

1 cohort genes are undrugged. Ranked by ‘starting-point quality’ (assay depth + drugged-partner adjacency).

SymbolChEMBL assaysDrugged partners (top 3)
CEP190

Clinical trials & evidence

Clinical trials

Clinical trials: 0.