Paroxysmal nocturnal hemoglobinuria 1

disease
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Also known as paroxysmal nocturnal hemoglobinuria caused by mutation in PIGAparoxysmal nocturnal hemoglobinuria type 1paroxysmal nocturnal hemoglobinuria, somaticPIGA paroxysmal nocturnal hemoglobinuriaPNH1

Summary

Paroxysmal nocturnal hemoglobinuria 1 (MONDO:0010438) is a disease with 2 cohort genes.

At a glance

  • Cohort genes: 2
  • ClinVar variants: 21

Clinical features

No curated clinical features (Orphanet) for this disease.

Identifiers

Disease identifiers

FieldValue
Canonical nameparoxysmal nocturnal hemoglobinuria 1
Mondo IDMONDO:0010438
OMIM300818
UMLSC3806670
MedGen813000
GARD0024726
Is cancer (heuristic)no

Also known as: paroxysmal nocturnal hemoglobinuria 1 · paroxysmal nocturnal hemoglobinuria caused by mutation in PIGA · paroxysmal nocturnal hemoglobinuria caused by mutation in pIgA · paroxysmal nocturnal hemoglobinuria type 1 · paroxysmal nocturnal hemoglobinuria, somatic · PIGA paroxysmal nocturnal hemoglobinuria · pIgA paroxysmal nocturnal hemoglobinuria · PNH1

Data availability: 21 ClinVar variants.

Disease family

Classification path: disease › human disease › disease by body system or component › urinary system disorderkidney disorderproteinuria › hemoglobinuria › paroxysmal nocturnal hemoglobinuriaparoxysmal nocturnal hemoglobinuria 1

Related subtypes (1): paroxysmal nocturnal hemoglobinuria 2

Genetics & variants

GWAS landscape

No GWAS associations recorded — common-variant (GWAS) studies don’t cover this disease (typical for Mendelian / rare diseases). See the curated gene cohort and Mendelian overlap below.

Variant details and genetic-evidence tiers

ClinVar germline variants

21 retrieved; paginated sample, class counts are floors:

9 likely pathogenic, 4 conflicting classifications of pathogenicity, 4 uncertain significance, 2 pathogenic/likely pathogenic, 1 pathogenic, 1 benign/likely benign

ClinVarVariant (HGVS)GeneClassificationReview
41400NC_000003.12:g.169765160G>CLOC110806306Pathogenicno assertion criteria provided
132814NM_002641.4(PIGA):c.355C>T (p.Arg119Trp)PIGAPathogenic/Likely pathogeniccriteria provided, multiple submitters, no conflicts
623369NM_002641.4(PIGA):c.145G>A (p.Val49Met)PIGAPathogenic/Likely pathogeniccriteria provided, multiple submitters, no conflicts
1033523NM_002641.4(PIGA):c.986T>C (p.Val329Ala)PIGALikely pathogeniccriteria provided, multiple submitters, no conflicts
1685404NM_002641.4(PIGA):c.109A>G (p.Met37Val)PIGALikely pathogeniccriteria provided, multiple submitters, no conflicts
2444337NM_002641.4(PIGA):c.1281_1282del (p.Phe428fs)PIGALikely pathogeniccriteria provided, single submitter
2501811NM_002641.4(PIGA):c.1188+1G>CPIGALikely pathogenicno assertion criteria provided
2502420NM_002641.4(PIGA):c.196_206del (p.Lys66fs)PIGALikely pathogenicno assertion criteria provided
2502425NM_002641.4(PIGA):c.151_187del (p.Ser51fs)PIGALikely pathogenicno assertion criteria provided
2502426NM_002641.4(PIGA):c.329dup (p.Pro111fs)PIGALikely pathogenicno assertion criteria provided
2502427NM_002641.4(PIGA):c.1139del (p.Ile380fs)PIGALikely pathogenicno assertion criteria provided
973228NM_002641.4(PIGA):c.1355A>T (p.Asp452Val)PIGALikely pathogeniccriteria provided, single submitter
1549539NM_002641.4(PIGA):c.849-19C>TPIGAConflicting classifications of pathogenicitycriteria provided, conflicting classifications
208742NM_002641.4(PIGA):c.98A>G (p.His33Arg)PIGAConflicting classifications of pathogenicitycriteria provided, conflicting classifications
432113NM_002641.4(PIGA):c.368C>T (p.Thr123Met)PIGAConflicting classifications of pathogenicitycriteria provided, conflicting classifications
625990NM_002641.4(PIGA):c.248T>C (p.Leu83Pro)PIGAConflicting classifications of pathogenicitycriteria provided, conflicting classifications
2502424NM_002641.4(PIGA):c.167T>C (p.Leu56Pro)PIGAUncertain significanceno assertion criteria provided
2502428NM_002641.4(PIGA):c.142G>A (p.Gly48Ser)PIGAUncertain significanceno assertion criteria provided
471950NM_002641.4(PIGA):c.1048C>T (p.Pro350Ser)PIGAUncertain significancecriteria provided, multiple submitters, no conflicts
548620NM_015937.6(PIGT):c.602T>C (p.Leu201Pro)PIGTUncertain significancecriteria provided, single submitter
471952NM_002641.4(PIGA):c.525T>C (p.Leu175=)PIGABenign/Likely benigncriteria provided, multiple submitters, no conflicts

Genes & proteins

Mendelian disease overlap and somatic drivers

GenCC: 0 · Orphanet: 6 · OMIM-shared: 0 · Dual-evidence (GWAS+Mendelian): 0

Orphanet rare-disease linkage (cohort genes)

GeneOrphanet IDRare disease
PIGTOrphanet:369837Intellectual disability-seizures-hypophosphatasia-ophthalmic-skeletal anomalies syndrome
PIGAOrphanet:293181Epilepsy of infancy with migrating focal seizures
PIGAOrphanet:300496Multiple congenital anomalies-hypotonia-seizures syndrome type 2
PIGAOrphanet:397922Ferro-cerebro-cutaneous syndrome
PIGAOrphanet:447Paroxysmal nocturnal hemoglobinuria
PIGAOrphanet:697160Infantile epileptic spasms syndrome

Cohort genes → proteins

2 cohort genes, 2 distinct canonical proteins.

Evidence partition

SubsetGenes
multi_evidence2

Cohort genes (full)

SymbolHGNCEnsemblUniProtNameEvidence
PIGTHGNC:14938ENSG00000124155Q969N2GPI-anchor transamidase component PIGTclinvar
PIGAHGNC:8957ENSG00000165195P37287Phosphatidylinositol N-acetylglucosaminyltransferase subunit Aclinvar

Cohort function summary

Lead sentence per gene, UniProt-curated.

SymbolProtein nameFunction (lead sentence)
PIGTGPI-anchor transamidase component PIGTComponent of the glycosylphosphatidylinositol-anchor (GPI-anchor) transamidase (GPI-T) complex that catalyzes the formation of the linkage between a proprotein and a GPI-anchor and participates in GPI anchored protein biosynthesis.
PIGAPhosphatidylinositol N-acetylglucosaminyltransferase subunit ACatalytic subunit of the glycosylphosphatidylinositol-N-acetylglucosaminyltransferase (GPI-GnT) complex that catalyzes the transfer of N-acetylglucosamine from UDP-N-acetylglucosamine to phosphatidylinositol and participates in the first s…

Protein-family classification

Druggable: 0 · Difficult: 0 · Unknown: 2 · Druggable fraction: 0.0

Family distribution

Cohort families vs a genome-wide background (hypergeometric, BH-FDR; fold = observed/expected). Counts kept; sorted by enrichment, so the catch-all Other/Unknown bucket no longer leads.

FamilyGenesFoldFDR
Other/Unknown21.8×0.312

Per-gene assignment

SymbolFamilyDruggable?ECInterPro (top 3)
PIGTOther/UnknownnoPIG-T
PIGAOther/UnknownnoGlyco_trans_1, PIGA_GPI_anchor_biosynthesis, PIG-A/GPI3

Expression context

Cohort genes with no expression data: 0.

2 cohort genes are a single-cell marker in ≥1 SCXA experiment.

Breadth distribution (Bgee present_calls)

BucketGenes
narrow (1-5 tissues)0
moderate (6-20)0
broad (>20)2
unknown0

Top tissues across cohort

TissueCohort genes
cardia of stomach1
pylorus1
stromal cell of endometrium1
endometrium epithelium1
mucosa of stomach1
secondary oocyte1

Per-gene tissue summary (top 30)

SymbolBgee breadthFANTOM5 breadthSCXATop tissues
PIGT253ubiquitousmarkercardia of stomach, stromal cell of endometrium, pylorus
PIGA266ubiquitousmarkersecondary oocyte, mucosa of stomach, endometrium epithelium

Protein interactions among cohort

Intra-cohort edges: 1.

Hub genes (top 10 by interactor count)

SymbolInteractor count
PIGA2,324
PIGT1,295

Intra-cohort edges

ABSources
PIGAPIGTstring_interaction

Structural data

PDB: 1 · AlphaFold-only: 1 · No structure: 0

Cohort genes with PDB structures (top 30)

SymbolUniProtPDB entries
PIGTQ969N24

AlphaFold-only cohort genes (top 30 by pLDDT)

SymbolUniProtpLDDT
PIGAP3728786.22

Function

Pathway analysis

Distinct Reactome pathways touched by cohort: 2. Enrichment computed across 2 evidence-associated genes (2 with Reactome annotation).

Pathways by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 2 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

PathwayCohort genesFoldFDRSample cohort genes
Attachment of GPI anchor to uPAR1634.4×0.003PIGT
Synthesis of glycosylphosphatidylinositol (GPI)1317.2×0.003PIGA

GO biological processes by enrichment

Over-representation of cohort genes vs the genome-wide background (hypergeometric test, Benjamini-Hochberg FDR; fold = observed/expected over 2 annotated cohort genes). Counts and members are kept as ground-truth; sorted by enrichment.

GO termCohort genesFoldFDRSample cohort genes
GPI anchor biosynthetic process2495.6×2e-05PIGT, PIGA
GPI anchored protein biosynthesis11404.3×0.002PIGT
attachment of GPI anchor to protein11053.2×0.002PIGT
neuron apoptotic process192.6×0.015PIGT
cellular response to leukemia inhibitory factor179.5×0.015PIGA
neuron differentiation150.1×0.020PIGT

Therapeutics

Drug target analysis

Approved (phase 4): 0 · Phase ≥3: 0 · Phased (≥1): 0 · Undrugged: 2

Druggability breadth: 1 of 2 evidence-associated genes (50%) have a ChEMBL target (buckets above are over the deeply-mined display cohort).

Top cohort targets by molecule count

SymbolMoleculesMax phase
PIGT00
PIGA00

Bioactivity and enzyme data

Enzyme cohort genes (≥1 EC): 0.

Cohort genes with ChEMBL bioactivity (full, sorted by assay count)

SymbolAssaysType breakdown
PIGT1Binding:1

Pharmacogenomics

Cohort genes with a PharmGKB record: 2; with CPIC/DPWG dosing guidelines: 0.

No cohort gene has a CPIC/DPWG genotype-guided dosing guideline (PharmGKB).

Chemical tractability of cohort targets

0 approved/phased compounds have measured bioactivity against a cohort gene (and aren’t yet in disease-level trials). This is a research / tractability signal, NOT a therapeutic recommendation — a bioactivity row often reflects off-target or screening binding (e.g. promiscuous kinase inhibitors against a cohort kinase), implying no disease mechanism.

Druggability pyramid

Cohort genes binned by druggability tier (high → low):

TierDefinitionGenesSymbols
AApproved (phase 4 drug)0
BPhased (≥1) drug, not yet approved0
CDruggable family + PDB, no drug0
DDruggable family + AlphaFold only, no drug0
EDifficult family or no structure, no drug2PIGT, PIGA

Undrugged target profiles

2 cohort genes are undrugged. Ranked by ‘starting-point quality’ (assay depth + drugged-partner adjacency).

SymbolChEMBL assaysDrugged partners (top 3)
PIGT1
PIGA0

Clinical trials & evidence

Clinical trials

Clinical trials: 0.