Progressive multifocal leukoencephalopathy

disease
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Also known as leukoencephalopathy, progressive multifocalPMLprogressive multifocal leukoencephalitis

Summary

Progressive multifocal leukoencephalopathy (MONDO:0016318) is a disease and 24 clinical trials. Top therapeutic interventions include cidofovir anhydrous, brincidofovir, and didanosine. A subtype of infectious encephalitis — broader associated-gene and molecular evidence is on the parent page (see Disease family below).

At a glance

  • Prevalence: <1 / 1 000 000 (Sweden) [Orphanet-validated]
  • Phenotypes (HPO): 35
  • Clinical trials: 24

Clinical features

Epidemiology

Prevalence records

2 prevalence record(s), Orphanet:

TypeClassValueGeographyValidation
Annual incidence<1 / 1 000 0000.068SwedenValidated
Annual incidence1-9 / 1 000 0000.11FranceValidated

Signs & symptoms

Clinical features (HPO)

35 HPO clinical features (Orphanet curated; top 35 by frequency):

HPO IDTermFrequency
HP:0000707Abnormality of the nervous systemVery frequent (80-99%)
HP:0002721ImmunodeficiencyVery frequent (80-99%)
HP:0002921Abnormality of the cerebrospinal fluidVery frequent (80-99%)
HP:0004302Functional motor deficitVery frequent (80-99%)
HP:0007305CNS demyelinationVery frequent (80-99%)
HP:0031392Abnormal proportion of CD4 T cellsVery frequent (80-99%)
HP:0100706Abnormality of the oligodendrogliaVery frequent (80-99%)
HP:0100707Abnormal astrocyte morphologyVery frequent (80-99%)
HP:0000505Visual impairmentFrequent (30-79%)
HP:0001260DysarthriaFrequent (30-79%)
HP:0001268Mental deteriorationFrequent (30-79%)
HP:0002066Gait ataxiaFrequent (30-79%)
HP:0002167Abnormality of speech or vocalizationFrequent (30-79%)
HP:0002315HeadacheFrequent (30-79%)
HP:0003474Somatic sensory dysfunctionFrequent (30-79%)
HP:0003690Limb muscle weaknessFrequent (30-79%)
HP:0004374Hemiplegia/hemiparesisFrequent (30-79%)
HP:0005415Decreased proportion of CD8-positive T cellsFrequent (30-79%)
HP:0010549Weakness due to upper motor neuron dysfunctionFrequent (30-79%)
HP:0100543Cognitive impairmentFrequent (30-79%)
HP:0000639NystagmusOccasional (5-29%)
HP:0000751Personality changesOccasional (5-29%)
HP:0001123Visual field defectOccasional (5-29%)
HP:0001250SeizureOccasional (5-29%)
HP:0001300ParkinsonismOccasional (5-29%)
HP:0002321VertigoOccasional (5-29%)
HP:0002381AphasiaOccasional (5-29%)
HP:0004377Hematological neoplasmOccasional (5-29%)
HP:0012246Oculomotor nerve palsyOccasional (5-29%)
HP:0025479Self-neglectOccasional (5-29%)
HP:0030516Homonymous hemianopiaOccasional (5-29%)
HP:0000651DiplopiaVery rare (<1-4%)
HP:0001287MeningitisVery rare (<1-4%)
HP:0001310DysmetriaVery rare (<1-4%)
HP:0003401ParesthesiaVery rare (<1-4%)

Identifiers

Disease identifiers

FieldValue
Canonical nameprogressive multifocal leukoencephalopathy
Mondo IDMONDO:0016318
EFOEFO:0007455
MeSHD007968
Orphanet217260
DOIDDOID:643
ICD-10-CMA81.2
ICD-11902939755
NCITC26815
SNOMED CT22255007
UMLSC0023524
MedGen7327
GARD0007468
MedDRA10036807
NORD1616
Is cancer (heuristic)no

Also known as: leukoencephalopathy, progressive multifocal · PML · progressive multifocal leukoencephalitis

Data availability: 5 cell lines.

Disease family

This is a subtype of infectious encephalitis. Genetic, therapeutic, and trial evidence is largely curated at the broader-term level — see the parent page for the associated-gene cohort and molecular evidence.

Classification path: disease › human disease › disease by body system or component › nervous system disordercentral nervous system disorderencephalomyelitisencephalitisinfectious encephalitisprogressive multifocal leukoencephalopathy

Related subtypes (9): primary amebic meningoencephalitis, granulomatous amebic encephalitis, syphilitic encephalitis, Kluver-Bucy syndrome, viral encephalitis, acute necrotizing encephalopathy of childhood, Hendra virus infection, Mycoplasma encephalitis, postinfectious encephalitis

Genetics & variants

GWAS landscape

No GWAS associations recorded — common-variant (GWAS) studies don’t cover this disease (typical for Mendelian / rare diseases). See the curated gene cohort and Mendelian overlap below.

Variant details and genetic-evidence tiers

No tiered GWAS variants or ClinVar records for this disease.

Genes & proteins

No associated-gene cohort resolved for this disease. Atlas builds the molecular and therapeutic sections — associated genes, protein families, druggability, pathways, interactions, and drug associations — by aggregating over a disease’s associated genes (resolved via GWAS / GenCC / ClinVar / CIViC), and none resolved here. This is expected for antibody-mediated, autoimmune, or otherwise non-gene-defined conditions; the curated evidence for this disease is its clinical features, GWAS susceptibility, and clinical trials (above).

Function

No pathway enrichment — requires an associated-gene cohort.

Therapeutics

Drugs indicated or in trials for this disease

No drug has an approved disease-direct ChEMBL indication for this disease.

1 drug in clinical trials for this disease (phase 2–3, investigational): efficacy not established — a trial record, not an indication.

DrugHighest phase
PembrolizumabPhase 2

Clinical trials & evidence

Clinical trials

Clinical trials: 24.

Phase distribution (across all retrieved trials)

PhaseTrials
Not specified12
PHASE26
EARLY_PHASE12
PHASE41
PHASE2/PHASE31
PHASE1/PHASE21
PHASE11

Top trials by phase / activity

NCTPhaseStatusTitle
NCT01211665PHASE4TERMINATEDCorticosteroids for Immune Reconstitution Inflammatory Syndrome (IRIS)
NCT06276504PHASE2/PHASE3NOT_YET_RECRUITINGPembrolizumab in Progressive Multifocal Leukoencephalopathy (PML) in Immunocompromised Patients Without HIV Infection
NCT07511049PHASE2RECRUITINGIntravenous Brincidofovir as an Antiviral for Treatment of Progressive Multifocal Leukoencephalopathy: A Pilot Study
NCT00001048PHASE2COMPLETEDComparison of Anti HIV Drugs Used Alone or in Combination With Cytosine Arabinoside to Treat Progressive Multifocal Leukoencephalopathy (PML) in HIV-Infected Patients
NCT00002395PHASE2COMPLETEDSafety and Effectiveness of Topotecan HCl to Treat HIV-Infected Patients With AIDS-Related Progressive Multifocal Leukoencephalopathy (PML)
NCT00120367PHASE2COMPLETEDEarly Intensification of Antiretroviral Therapy Including Enfuvirtide in HIV-1-Related Progressive Multifocal Leucoencephalopathy (ANRS125)
NCT00746941PHASE1/PHASE2TERMINATEDStudy to Explore the Effect of Mefloquine in Participants With Progressive Multifocal Leukoencephalopathy (PML)
NCT04091932PHASE2UNKNOWNTreatment of PD-1 Inhibitor in AIDS-associated PML
NCT05541549PHASE2UNKNOWNA Phase 2 Study Evaluating JCPyV-specific T Cell Therapy for PML
NCT05849467PHASE1RECRUITINGCentral Nervous System Uptake of Anti-CD8+ T Cell Minibodies in Multiple Sclerosis and Progressive Multifocal Leukoencephalopathy
NCT02694783EARLY_PHASE1COMPLETEDAdoptive Cellular Immunotherapy for Progressive Multifocal Leukoencephalopathy With Ex Vivo Generated Polyomavirus-Specific T-Cells
NCT04781309EARLY_PHASE1COMPLETEDNT-I7, a Long-Acting Recombinant IL-7 Molecule, as an Immune Reconstitution Strategy for Lymphopenia in Patients With Progressive Multifocal Leukoencephalopathy
NCT01730131Not specifiedRECRUITINGNatural History Study of Progressive Multifocal Leukoencephalopathy (PML)
NCT07512518Not specifiedRECRUITINGObservational Cohort Study of Chronic Viral Infection in the Central Nervous System
NCT00000945Not specifiedCOMPLETEDA Study to Evaluate the Use of Cidofovir (an Experimental Drug) for the Treatment of Progressive Multifocal Leukoencephalopathy (PML) in AIDS Patients
NCT00002270Not specifiedCOMPLETEDA Pilot Study of the Efficacy of Recombinant Alpha Interferon (IFN-A2b) and Zidovudine (AZT) in the Treatment of Progressive Multifocal Leukoencephalopathy (PML) Complicating HIV-1 Infection
NCT00002274Not specifiedCOMPLETEDA Study of ddI in Patients With AIDS Who Become Sicker While Taking Zidovudine
NCT01132053Not specifiedCOMPLETEDRole of Inflammation in Progressive Multifocal Leukoencephalopathy (PML)
NCT01211639Not specifiedTERMINATEDGenetic Evaluation of Natalizumab-Treated Patients With Progressive Multifocal Leukoencephalopathy
NCT02004444Not specifiedCOMPLETEDJC Virus Reactivation in Multiple Sclerosis
NCT02895581Not specifiedCOMPLETEDRetrospective Study of the Survival of Patients Suffering From Hiv-related Progressive Multifocal Leukoencephalopathy
NCT03399981Not specifiedCOMPLETEDTysabri Observational Cohort Study - Multiple Sclerosis (MS) Registries
NCT04453917Not specifiedCOMPLETEDDynamics of T Cell Expression of Immune Checkpoint Molecules in Progressive Multifocal Leukoencephalopathy
NCT06594614Not specifiedCOMPLETEDObservational Study on Characteristics and Survival Correlates of Progressive Multifocal Leukoencephalopathy (PML) in Italy

Drugs tested across these trials (top 30)

MoleculeMax phaseTrials referencing
CIDOFOVIR ANHYDROUS42
BRINCIDOFOVIR41
DIDANOSINE41
ENFUVIRTIDE41
INTERFERON ALFA-2B41
MEFLOQUINE41
METHYLPREDNISOLONE41
NATALIZUMAB41
PREDNISOLONE41
PROBENECID41
TOPOTECAN41
ZALCITABINE41
EFINEPTAKIN ALFA21
CHEMBL3906601
(S,R)-MEFLOQUINE01